Correlation of X chromosome inactivation with clinical presentation of Fabry disease in a case report Correlación de la inactivación del cromosoma X con la presentación clínica de la enfermedad de Fabry a propósito de un caso

Fabry disease or also called Anderson-Fabry disease (FD) is a rare disease caused by pathogenic variants in the GLA gene, located on the X chromosome. This gene is involved in the metabolism of glycosphingolipids and its pathogenic variants cause a deficit or absence of α-galactosidase A causing the...

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Detalles Bibliográficos
Autores: Rodríguez Doyágüez, Pablo|||0000-0001-6196-7416, Furlano, Monica|||0000-0003-1025-3901, Ars, Elisabet|||0000-0002-4118-4358, Arce, Yolanda, Guirado, Luis|||0000-0001-5119-3912, Torra Balcells, Roser|||0000-0001-8714-2332
Tipo de recurso: artículo
Fecha de publicación:2023
País:España
Institución:Universitat Autònoma de Barcelona
Repositorio:Dipòsit Digital de Documents de la UAB
Idioma:español
OAI Identifier:oai:ddd.uab.cat:303863
Acceso en línea:https://ddd.uab.cat/record/303863
https://dx.doi.org/urn:doi:10.1016/j.nefro.2022.12.001
Access Level:acceso abierto
Palabra clave:Fabry
Globotriaosilceramida
Globotriaosylceramide
Lionización
Lionization
α-Galactosidase A
α-galactosidase A
Descripción
Sumario:Fabry disease or also called Anderson-Fabry disease (FD) is a rare disease caused by pathogenic variants in the GLA gene, located on the X chromosome. This gene is involved in the metabolism of glycosphingolipids and its pathogenic variants cause a deficit or absence of α-galactosidase A causing the deposition of globotriaosylceramide throughout the body. Females have a variable phenotypic expression and a better prognosis than males. This is due to the X chromosome inactivation phenomenon. We present a clinical case of Fabry disease in a female with predominantly renal involvement and demonstrate how the X chromosome inactivation phenomenon is tissue dependent, showing preferential inactivation of the mutated allele at the renal level.