Consolidation deficits in episodic memory define distinct clinical and neurodegenerative profiles in Huntington's disease

Background: Huntington's disease (HD) is primarily associated with executive dysfunction, but episodic memory impairment is also present. Traditionally, these memory deficits have been attributed to retrieval difficulties linked to fronto-striatal dysfunction, rather than to disruptions in enco...

Descripción completa

Detalles Bibliográficos
Autores: Martínez-Horta, Saul|||0000-0003-0125-7249, Quevedo-García, Angela, Puig-Davi, Arnau|||0000-0001-8883-4947, Sampedro, Frederic|||0000-0002-3933-1355, Oltra-Cucarella, Javier, Pérez-Pérez, Jesús|||0000-0002-9835-0484, Franch-Martí, Carla, Olmedo-Saura, Gonzalo|||0000-0003-4864-5548, Rivas Asensio, Elisa, Vázquez-Oliver, Anna|||0000-0002-9842-7656, Pérez-Carasol, Laura, Horta-Barba, Andrea|||0000-0003-0050-5466, Pagonabarraga Mora, Javier|||0000-0002-3248-704X, Kulisevsky, Jaime|||0000-0003-4870-1431
Tipo de recurso: artículo
Fecha de publicación:2025
País:España
Institución:Universitat Autònoma de Barcelona
Repositorio:Dipòsit Digital de Documents de la UAB
Idioma:inglés
OAI Identifier:oai:dnet:uabarcelona_::d73ea89a4cb0735b707b8abee2375f56
Acceso en línea:https://ddd.uab.cat/record/326935
https://dx.doi.org/urn:doi:10.1016/j.nicl.2025.103894
Access Level:acceso abierto
Palabra clave:Huntington's disease
Neuropsychology
Episodic memory
Hippocampus
MRI
Descripción
Sumario:Background: Huntington's disease (HD) is primarily associated with executive dysfunction, but episodic memory impairment is also present. Traditionally, these memory deficits have been attributed to retrieval difficulties linked to fronto-striatal dysfunction, rather than to disruptions in encoding or consolidation processes. However, the specific nature and diversity of memory impairments in HD remain underexplored. Objective: To characterize the profile of episodic memory impairment in HD, identify distinct cognitive phenotypes, and examine their clinical, neuroanatomical, and biomarker correlates. Methods: We assessed episodic memory in HD patients and healthy controls using the Free and Cued Selective Reminding Test (FCSRT), complemented by Item-Specific Deficit Approach (ISDA) indices to quantify encoding, consolidation, and retrieval deficits. Structural MRI was used to identify gray matter volume correlates, and plasma neurofilament light chain (NfL) was measured as a marker of neuroaxonal injury. Results: Compared to controls, HD patients showed marked impairments in free recall with preserved cued recall, suggesting predominant retrieval deficits. However, nearly one-third of patients exhibited global impairments across all FCSRT components, mainly driven by consolidation deficits consistent with medial temporal lobe dysfunction. This subgroup also showed worse cognitive and functional performance and significant atrophy in the hippocampus, entorhinal cortex, and parahippocampal gyrus.