Comprehensive custom ngs panel validation for the improvement of the stratification of b-acute lymphoblastic leukemia patients

© 2020 by the authors.

Detalles Bibliográficos
Autores: Montaño, Adrián, Hernandez-Sánchez, Jesus M., Forero-Castro, Maribel, Matorra-Miguel, María, Lumbreras, Eva, Miguel, Cristina, Santos-Mínguez, Sandra, Ramírez-Maldonado, Valentina, Fuster, José Luis, Heras, Natalia de las, García de Coca, Alfonso, Sierra, Magdalena, Dávila, Julio, Fuente, Ignacio de la, Olivier, Carmen, Olazabal, Juan, Martínez, Joaquín, Vega-García, Nerea, González, Teresa, Hernández, Jesús M., Benito, Rocío
Tipo de recurso: artículo
Estado:Versión publicada
Fecha de publicación:2020
País:España
Institución:Consejo Superior de Investigaciones Científicas (CSIC)
Repositorio:DIGITAL.CSIC. Repositorio Institucional del CSIC
OAI Identifier:oai:digital.csic.es:10261/226481
Acceso en línea:http://hdl.handle.net/10261/226481
Access Level:acceso abierto
Palabra clave:Acute lymphoblastic leukemia
NGS
Genetic alterations
Diagnosis
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dc.title.none.fl_str_mv Comprehensive custom ngs panel validation for the improvement of the stratification of b-acute lymphoblastic leukemia patients
title Comprehensive custom ngs panel validation for the improvement of the stratification of b-acute lymphoblastic leukemia patients
spellingShingle Comprehensive custom ngs panel validation for the improvement of the stratification of b-acute lymphoblastic leukemia patients
Montaño, Adrián
Acute lymphoblastic leukemia
NGS
Genetic alterations
Diagnosis
title_short Comprehensive custom ngs panel validation for the improvement of the stratification of b-acute lymphoblastic leukemia patients
title_full Comprehensive custom ngs panel validation for the improvement of the stratification of b-acute lymphoblastic leukemia patients
title_fullStr Comprehensive custom ngs panel validation for the improvement of the stratification of b-acute lymphoblastic leukemia patients
title_full_unstemmed Comprehensive custom ngs panel validation for the improvement of the stratification of b-acute lymphoblastic leukemia patients
title_sort Comprehensive custom ngs panel validation for the improvement of the stratification of b-acute lymphoblastic leukemia patients
dc.creator.none.fl_str_mv Montaño, Adrián
Hernandez-Sánchez, Jesus M.
Forero-Castro, Maribel
Matorra-Miguel, María
Lumbreras, Eva
Miguel, Cristina
Santos-Mínguez, Sandra
Ramírez-Maldonado, Valentina
Fuster, José Luis
Heras, Natalia de las
García de Coca, Alfonso
Sierra, Magdalena
Dávila, Julio
Fuente, Ignacio de la
Olivier, Carmen
Olazabal, Juan
Martínez, Joaquín
Vega-García, Nerea
González, Teresa
Hernández, Jesús M.
Benito, Rocío
author Montaño, Adrián
author_facet Montaño, Adrián
Hernandez-Sánchez, Jesus M.
Forero-Castro, Maribel
Matorra-Miguel, María
Lumbreras, Eva
Miguel, Cristina
Santos-Mínguez, Sandra
Ramírez-Maldonado, Valentina
Fuster, José Luis
Heras, Natalia de las
García de Coca, Alfonso
Sierra, Magdalena
Dávila, Julio
Fuente, Ignacio de la
Olivier, Carmen
Olazabal, Juan
Martínez, Joaquín
Vega-García, Nerea
González, Teresa
Hernández, Jesús M.
Benito, Rocío
author_role author
author2 Hernandez-Sánchez, Jesus M.
Forero-Castro, Maribel
Matorra-Miguel, María
Lumbreras, Eva
Miguel, Cristina
Santos-Mínguez, Sandra
Ramírez-Maldonado, Valentina
Fuster, José Luis
Heras, Natalia de las
García de Coca, Alfonso
Sierra, Magdalena
Dávila, Julio
Fuente, Ignacio de la
Olivier, Carmen
Olazabal, Juan
Martínez, Joaquín
Vega-García, Nerea
González, Teresa
Hernández, Jesús M.
Benito, Rocío
author2_role author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
dc.contributor.none.fl_str_mv Junta de Castilla y León
Fundación Castellano Leonesa de Hematología y Hemoterapia
Centro de Investigación Biomédica en Red Cáncer (España)
Instituto de Salud Carlos III
Asociación Española Contra el Cáncer
Consejo Superior de Investigaciones Científicas [https://ror.org/02gfc7t72]
dc.subject.none.fl_str_mv Acute lymphoblastic leukemia
NGS
Genetic alterations
Diagnosis
topic Acute lymphoblastic leukemia
NGS
Genetic alterations
Diagnosis
description © 2020 by the authors.
publishDate 2020
dc.date.none.fl_str_mv 2020
2021
2021
2021
dc.type.none.fl_str_mv info:eu-repo/semantics/article
http://purl.org/coar/resource_type/c_6501
Publisher's version
info:eu-repo/semantics/publishedVersion
format article
status_str publishedVersion
dc.identifier.none.fl_str_mv http://hdl.handle.net/10261/226481
url http://hdl.handle.net/10261/226481
dc.language.none.fl_str_mv Inglés
language_invalid_str_mv Inglés
dc.relation.none.fl_str_mv http://dx.doi.org/10.3390/jpm10030137

dc.rights.none.fl_str_mv info:eu-repo/semantics/openAccess
eu_rights_str_mv openAccess
dc.publisher.none.fl_str_mv Multidisciplinary Digital Publishing Institute
publisher.none.fl_str_mv Multidisciplinary Digital Publishing Institute
dc.source.none.fl_str_mv reponame:DIGITAL.CSIC. Repositorio Institucional del CSIC
instname:Consejo Superior de Investigaciones Científicas (CSIC)
instname_str Consejo Superior de Investigaciones Científicas (CSIC)
reponame_str DIGITAL.CSIC. Repositorio Institucional del CSIC
collection DIGITAL.CSIC. Repositorio Institucional del CSIC
repository.name.fl_str_mv
repository.mail.fl_str_mv
_version_ 1869413639181565952
spelling Comprehensive custom ngs panel validation for the improvement of the stratification of b-acute lymphoblastic leukemia patientsMontaño, AdriánHernandez-Sánchez, Jesus M.Forero-Castro, MaribelMatorra-Miguel, MaríaLumbreras, EvaMiguel, CristinaSantos-Mínguez, SandraRamírez-Maldonado, ValentinaFuster, José LuisHeras, Natalia de lasGarcía de Coca, AlfonsoSierra, MagdalenaDávila, JulioFuente, Ignacio de laOlivier, CarmenOlazabal, JuanMartínez, JoaquínVega-García, NereaGonzález, TeresaHernández, Jesús M.Benito, RocíoAcute lymphoblastic leukemiaNGSGenetic alterationsDiagnosis© 2020 by the authors.[Background]: B-acute lymphoblastic leukemia (B-ALL) is a hematological neoplasm of the stem lymphoid cell of the B lineage, characterized by the presence of genetic alterations closely related to the course of the disease. The number of alterations identified in these patients grows as studies of the disease progress, but in clinical practice, the conventional techniques frequently used are only capable of detecting the most common alterations. However, techniques, such as next-generation sequencing (NGS), are being implemented to detect a wide spectrum of new alterations that also include point mutations. Methods: In this study, we designed and validated a comprehensive custom NGS panel to detect the main genetic alterations present in the disease in a single step. For this purpose, 75 B-ALL diagnosis samples from patients previously characterized by standard-of-care diagnostic techniques were sequenced. [Results]: The use of the custom NGS panel allowed the correct detection of the main genetic alterations present in B-ALL patients, including the presence of an aneuploid clone in 14 of the samples and some of the recurrent fusion genes in 35 of the samples. The panel was also able to successfully detect a number of secondary alterations, such as single nucleotide variants (SNVs) and copy number variations (CNVs) in 66 and 46 of the samples analyzed, respectively, allowing for further refinement of the stratification of patients. The custom NGS panel could also detect alterations with a high level of sensitivity and reproducibility when the findings obtained by NGS were compared with those obtained from other conventional techniques. [Conclusions]: The use of this custom NGS panel allows us to quickly and efficiently detect the main genetic alterations present in B-ALL patients in a single assay (SNVs and insertions/deletions (INDELs), recurrent fusion genes, CNVs, aneuploidies, and single nucleotide polymorphisms (SNPs) associated with pharmacogenetics). The application of this panel would thus allow us to speed up and simplify the molecular diagnosis of patients, helping patient stratification and management.This work was financially supported in part by a grant from the Consejería de Educación, Junta de Castilla y León, Fondos FEDER (SA085U16, SA271P18), and the Regional Council of Castilla y León SACYL, (GRS 2062/A/19, GRS 1847/A/18), Fundación Castellano Leonesa de Hematología y Hemoterapia (FUCALHH 2017), Proyectos de Investigación en Biomedicina, Gestión Sanitaria y Atención Sociosanitaria del IBSAL (IBY17/00006), Centro de Investigación Biomédica en Red de Cáncer (CIBERONC CB16/12/00233), SYNtherapy. Synthetic Lethality for Personalized Therapy-based Stratification In Acute Leukemia (ERAPERMED2018-275); ISCIII (AC18/00093), co-funded by ERDF/ESF, “Investing in your future” and a grant to AM from the Junta Provincial de Salamanca of the Asociación Española Contra el Cáncer (AECC).Multidisciplinary Digital Publishing InstituteJunta de Castilla y LeónFundación Castellano Leonesa de Hematología y HemoterapiaCentro de Investigación Biomédica en Red Cáncer (España)Instituto de Salud Carlos IIIAsociación Española Contra el CáncerConsejo Superior de Investigaciones Científicas [https://ror.org/02gfc7t72]2021202120202021info:eu-repo/semantics/articlehttp://purl.org/coar/resource_type/c_6501Publisher's versioninfo:eu-repo/semantics/publishedVersionhttp://hdl.handle.net/10261/226481reponame:DIGITAL.CSIC. Repositorio Institucional del CSICinstname:Consejo Superior de Investigaciones Científicas (CSIC)Ingléshttp://dx.doi.org/10.3390/jpm10030137Síinfo:eu-repo/semantics/openAccessoai:digital.csic.es:10261/2264812026-05-22T06:33:51Z
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