Familial hypomagnesemia with hypercalciuria and nefrocalcinosis due to a mutation in the CLDN16 gen (Claudina 16). A case report

We report the case of a girl with a history of seizures associated with persistent severe hypomagnesemia, hypocalcemia, hypercalciuria,  accompanied by alterations in renal function, metabolic acidosis and Nephrocalcinosis with progression to stage 5 chronic kidney disease (CKD) with a fami...

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Detalhes bibliográficos
Autores: Loza Munarriz, Reyner, Arias Caceres, Fernando, Neyra Chagua, Victor
Formato: artículo
Estado:Versión publicada
Fecha de publicación:2024
País:Perú
Recursos:Universidad Peruana Cayetano Heredia
Repositorio:Revistas - Universidad Peruana Cayetano Heredia
Idioma:español
OAI Identifier:oai:revistas.upch.edu.pe:article/5335
Acesso em linha:https://revistas.upch.edu.pe/index.php/RMH/article/view/5335
Access Level:acceso abierto
Palavra-chave:Claudinas
deficiencia de magnesio
nefrocalcinosis
trasplante de riñón
hipocalcemia
Claudin
magnesium deficiency
nephrocalcinosis
kidney transplantation
hypocalcemia
Descrição
Resumo:We report the case of a girl with a history of seizures associated with persistent severe hypomagnesemia, hypocalcemia, hypercalciuria,  accompanied by alterations in renal function, metabolic acidosis and Nephrocalcinosis with progression to stage 5 chronic kidney disease (CKD) with a family history of chronic kidney disease, kidney stones and consanguinity of the parents, which is why the genetic study was carried out, resulting in a pathogenic mutation in homozygosity c.446 G>A (p.R149Q) located in exon 3 of the CLDN16 gene, which allows etiological diagnostic confirmation of a case of  Hypomagnesemia Familial with Hypercalciuria and Nephrocalcinosis (HFHNC), without severe ocular defects. In addition , the post-transplant evolution with good graft survival is presented.