Nivolumab and sunitinib in patients with advanced bone sarcomas: A multicenter, single-arm, phase 2 trial

[Background] Herein, we present the results of the phase 2 IMMUNOSARC study (NCT03277924), investigating sunitinib and nivolumab in adult patients with advanced bone sarcomas (BS).

Detalles Bibliográficos
Autores: Palmerini, Emanuela, Pousa, A. L., Grignani, Giovanni, Redondo, Andrés, Hindi, Nadia, Provenzano, Salvatore, Sebio, Ana, López-Martín, José A., Valverde, Claudia, Martínez-Trufero, Javier, Cea Gutiérrez, Antonio, Álava, Enrique de, Aparisi Gómez, María Pilar, D'Ambrosio, Lorenzo, Collini, Paola, Bazzocchi, Alberto, Moura, David S., Ibrahim, Toni, Stacchiotti, Silvia, Broto, Javier Martin
Tipo de recurso: artículo
Fecha de publicación:2025
País:España
Institución:Consejo Superior de Investigaciones Científicas (CSIC)
Repositorio:DIGITAL.CSIC. Repositorio Institucional del CSIC
OAI Identifier:oai:digital.csic.es:10261/390726
Acceso en línea:http://hdl.handle.net/10261/390726
https://api.elsevier.com/content/abstract/scopus_id/85208970345
Access Level:acceso abierto
Palabra clave:Ewing sarcoma
PD‐L1 inhibitor
Anti‐angiogeninic
Bone
Dedifferentiated chondrosarcoma
Immunotherapya
Nivolumab
Osteosarcoma
Sarcoma
Sunitinib
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spelling Nivolumab and sunitinib in patients with advanced bone sarcomas: A multicenter, single-arm, phase 2 trialPalmerini, EmanuelaPousa, A. L.Grignani, GiovanniRedondo, AndrésHindi, NadiaProvenzano, SalvatoreSebio, AnaLópez-Martín, José A.Valverde, ClaudiaMartínez-Trufero, JavierCea Gutiérrez, AntonioÁlava, Enrique deAparisi Gómez, María PilarD'Ambrosio, LorenzoCollini, PaolaBazzocchi, AlbertoMoura, David S.Ibrahim, ToniStacchiotti, SilviaBroto, Javier MartinEwing sarcomaPD‐L1 inhibitorAnti‐angiogeninicBoneDedifferentiated chondrosarcomaImmunotherapyaNivolumabOsteosarcomaPD‐L1 inhibitorSarcomaSunitinib[Background] Herein, we present the results of the phase 2 IMMUNOSARC study (NCT03277924), investigating sunitinib and nivolumab in adult patients with advanced bone sarcomas (BS).[Methods] Progressing patients with a diagnosis of BS were eligible. Treatment was comprised of sunitinib (37.5 mg/day on days 1–14, 25 mg/day afterword) plus nivolumab (3 mg/kg every 2 weeks). Primary end point was progression-free survival rate (PFSR) at 6 months based on central radiology review. Secondary end points were overall survival (OS), overall response rate (ORR) by Response Evaluation Criteria in Solid Tumors (RECIST) v1.1, and safety.[Results] A total of 46 patients were screened, 40 patients entered the study, and 38 underwent central radiological review and were evaluable for primary end point. Median age was 47 years (range, 21–74). Histologies include 17 (43%) osteosarcoma, 14 chondrosarcoma (35%, 10 conventional, four dedifferentiated [DDCS]), eight (20%) Ewing sarcoma, and one (2%) undifferentiated pleomorphic sarcoma. The PFSR at 6 months was 42% (95% confidence interval [CI], 27–58). With a median follow-up of 39.8 months (95% CI, 37.9–41.7), the median PFS and OS were 3.8 months (95% CI, 2.7–4.8) and 11.9 months (95% CI, 5.6–18.2). ORR by RECIST was 5%, with two of 38 partial responses (one of four DDCS and one of 17 osteosarcoma), 19 of 38 (50%) stable disease, and 17 of 38 (45%) progressions. Grade ≥3 adverse events were neutropenia (six of 40, 15%), anemia (5/40, hypertension (6/40, 15%), 12.5%), ALT/AST elevation (5/40, 12.5%), and pneumonitis (1/40, 2.5%). Seventeen percent of patients discontinued treatment due to toxicity, including a treatment-related grade 5 pneumonitis.[Conclusion] The trial met its primary end point in the BS cohort with >15% of patients progression-free at 6 months. However, the toxicity profile of this regimen was relevant.Bristol-Myers Squibb (BMS) and Pfizer provided drug supply and partial funding for logistics. This work was supported by the CARISBO Foundation Call for Translational and Clinical Medical Research. Open access funding provided by BIBLIOSAN.Peer reviewedWiley-VCHBristol-Myers SquibbPfizerFondazione CarisboBibliosanPalmerini, Emanuela [0000-0003-3406-6705]Martínez-Trufero, Javier [0000-0002-0997-2573]Stacchiotti, Silvia [0000-0002-1742-8666]Consejo Superior de Investigaciones Científicas [https://ror.org/02gfc7t72]202520252025info:eu-repo/semantics/articlehttp://purl.org/coar/resource_type/c_6501application/pdfhttp://hdl.handle.net/10261/390726https://api.elsevier.com/content/abstract/scopus_id/85208970345reponame:DIGITAL.CSIC. Repositorio Institucional del CSICinstname:Consejo Superior de Investigaciones Científicas (CSIC)InglésThe underlying dataset has been published as supplementary material of the article in the publisher platform at DOI http://dx.doi.org/10.1002/cncr.35628http://dx.doi.org/10.1002/cncr.35628Síinfo:eu-repo/semantics/openAccessoai:digital.csic.es:10261/3907262026-05-22T06:33:51Z
dc.title.none.fl_str_mv Nivolumab and sunitinib in patients with advanced bone sarcomas: A multicenter, single-arm, phase 2 trial
title Nivolumab and sunitinib in patients with advanced bone sarcomas: A multicenter, single-arm, phase 2 trial
spellingShingle Nivolumab and sunitinib in patients with advanced bone sarcomas: A multicenter, single-arm, phase 2 trial
Palmerini, Emanuela
Ewing sarcoma
PD‐L1 inhibitor
Anti‐angiogeninic
Bone
Dedifferentiated chondrosarcoma
Immunotherapya
Nivolumab
Osteosarcoma
PD‐L1 inhibitor
Sarcoma
Sunitinib
title_short Nivolumab and sunitinib in patients with advanced bone sarcomas: A multicenter, single-arm, phase 2 trial
title_full Nivolumab and sunitinib in patients with advanced bone sarcomas: A multicenter, single-arm, phase 2 trial
title_fullStr Nivolumab and sunitinib in patients with advanced bone sarcomas: A multicenter, single-arm, phase 2 trial
title_full_unstemmed Nivolumab and sunitinib in patients with advanced bone sarcomas: A multicenter, single-arm, phase 2 trial
title_sort Nivolumab and sunitinib in patients with advanced bone sarcomas: A multicenter, single-arm, phase 2 trial
dc.creator.none.fl_str_mv Palmerini, Emanuela
Pousa, A. L.
Grignani, Giovanni
Redondo, Andrés
Hindi, Nadia
Provenzano, Salvatore
Sebio, Ana
López-Martín, José A.
Valverde, Claudia
Martínez-Trufero, Javier
Cea Gutiérrez, Antonio
Álava, Enrique de
Aparisi Gómez, María Pilar
D'Ambrosio, Lorenzo
Collini, Paola
Bazzocchi, Alberto
Moura, David S.
Ibrahim, Toni
Stacchiotti, Silvia
Broto, Javier Martin
author Palmerini, Emanuela
author_facet Palmerini, Emanuela
Pousa, A. L.
Grignani, Giovanni
Redondo, Andrés
Hindi, Nadia
Provenzano, Salvatore
Sebio, Ana
López-Martín, José A.
Valverde, Claudia
Martínez-Trufero, Javier
Cea Gutiérrez, Antonio
Álava, Enrique de
Aparisi Gómez, María Pilar
D'Ambrosio, Lorenzo
Collini, Paola
Bazzocchi, Alberto
Moura, David S.
Ibrahim, Toni
Stacchiotti, Silvia
Broto, Javier Martin
author_role author
author2 Pousa, A. L.
Grignani, Giovanni
Redondo, Andrés
Hindi, Nadia
Provenzano, Salvatore
Sebio, Ana
López-Martín, José A.
Valverde, Claudia
Martínez-Trufero, Javier
Cea Gutiérrez, Antonio
Álava, Enrique de
Aparisi Gómez, María Pilar
D'Ambrosio, Lorenzo
Collini, Paola
Bazzocchi, Alberto
Moura, David S.
Ibrahim, Toni
Stacchiotti, Silvia
Broto, Javier Martin
author2_role author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
dc.contributor.none.fl_str_mv Bristol-Myers Squibb
Pfizer
Fondazione Carisbo
Bibliosan
Palmerini, Emanuela [0000-0003-3406-6705]
Martínez-Trufero, Javier [0000-0002-0997-2573]
Stacchiotti, Silvia [0000-0002-1742-8666]
Consejo Superior de Investigaciones Científicas [https://ror.org/02gfc7t72]
dc.subject.none.fl_str_mv Ewing sarcoma
PD‐L1 inhibitor
Anti‐angiogeninic
Bone
Dedifferentiated chondrosarcoma
Immunotherapya
Nivolumab
Osteosarcoma
PD‐L1 inhibitor
Sarcoma
Sunitinib
topic Ewing sarcoma
PD‐L1 inhibitor
Anti‐angiogeninic
Bone
Dedifferentiated chondrosarcoma
Immunotherapya
Nivolumab
Osteosarcoma
PD‐L1 inhibitor
Sarcoma
Sunitinib
description [Background] Herein, we present the results of the phase 2 IMMUNOSARC study (NCT03277924), investigating sunitinib and nivolumab in adult patients with advanced bone sarcomas (BS).
publishDate 2025
dc.date.none.fl_str_mv 2025
2025
2025
dc.type.none.fl_str_mv info:eu-repo/semantics/article
http://purl.org/coar/resource_type/c_6501
format article
dc.identifier.none.fl_str_mv http://hdl.handle.net/10261/390726
https://api.elsevier.com/content/abstract/scopus_id/85208970345
url http://hdl.handle.net/10261/390726
https://api.elsevier.com/content/abstract/scopus_id/85208970345
dc.language.none.fl_str_mv Inglés
language_invalid_str_mv Inglés
dc.relation.none.fl_str_mv The underlying dataset has been published as supplementary material of the article in the publisher platform at DOI http://dx.doi.org/10.1002/cncr.35628
http://dx.doi.org/10.1002/cncr.35628

dc.rights.none.fl_str_mv info:eu-repo/semantics/openAccess
eu_rights_str_mv openAccess
dc.format.none.fl_str_mv application/pdf
dc.publisher.none.fl_str_mv Wiley-VCH
publisher.none.fl_str_mv Wiley-VCH
dc.source.none.fl_str_mv reponame:DIGITAL.CSIC. Repositorio Institucional del CSIC
instname:Consejo Superior de Investigaciones Científicas (CSIC)
instname_str Consejo Superior de Investigaciones Científicas (CSIC)
reponame_str DIGITAL.CSIC. Repositorio Institucional del CSIC
collection DIGITAL.CSIC. Repositorio Institucional del CSIC
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repository.mail.fl_str_mv
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