Molecular Landscape and Validation of New Genomic Classification in 2668 Adult AML Patients: Real Life Data from the PETHEMA Registry

Simple Summary Next-Generation Sequencing (NGS) has provided a deeper genetic understanding of acute myeloid leukemia (AML) that has been recently incorporated into AML classification and risk-stratification guidelines. Single molecular analysis has become inefficient and molecular testing based on...

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Autores: Sargas, Claudia, Ayala, Rosa, Larrayoz, Maria Jose, Chillon, Maria Carmen, Carrillo-Cruz, Estrella, Bilbao-Sieyro, Cristina, Prados de la Torre, Esther, Martinez-Cuadron, David, Rodriguez-Veiga, Rebeca, Boluda, Blanca, Gil, Cristina, Bernal, Teresa, Bergua, Juan Miguel, Algarra, Lorenzo, Tormo, Mar, Martinez-Sanchez, Pilar, Soria, Elena, Serrano, Josefina, Alonso-Dominguez, Juan Manuel, Garcia-Boyero, Raimundo, Amigo, Maria Luz, Herrera-Puente, Pilar, Sayas, Maria Jose, Lavilla-Rubira, Esperanza, Martinez-Lopez, Joaquin, Calasanz, Maria Jose, Garcia-Sanz, Ramon, Perez-Simon, Jose Antonio, Gomez-Casares, Maria Teresa, Sanchez-Garcia, Joaquin, Barragan, Eva, Montesinos, Pau, On Behalf Of Pethema Group
Tipo de recurso: artículo
Estado:Versión publicada
Fecha de publicación:2023
País:España
Institución:INCLIVA
Repositorio:r-INCLIVA. Repositorio Institucional de Producción Científica de INCLIVA
OAI Identifier:oai:incliva.fundanetsuite.com:p17130
Acceso en línea:https://incliva.portalinvestigacion.com/publicaciones/17130
Access Level:acceso abierto
Palabra clave:acute myeloid leukemia
Next-Generation Sequencing
cross-validations
mutational profile
genomic classification
clinical validation
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spelling Molecular Landscape and Validation of New Genomic Classification in 2668 Adult AML Patients: Real Life Data from the PETHEMA RegistrySargas, ClaudiaAyala, RosaLarrayoz, Maria JoseChillon, Maria CarmenCarrillo-Cruz, EstrellaBilbao-Sieyro, CristinaPrados de la Torre, EstherMartinez-Cuadron, DavidRodriguez-Veiga, RebecaBoluda, BlancaGil, CristinaBernal, TeresaBergua, Juan MiguelAlgarra, LorenzoTormo, MarMartinez-Sanchez, PilarSoria, ElenaSerrano, JosefinaAlonso-Dominguez, Juan ManuelGarcia-Boyero, RaimundoAmigo, Maria LuzHerrera-Puente, PilarSayas, Maria JoseLavilla-Rubira, EsperanzaMartinez-Lopez, JoaquinCalasanz, Maria JoseGarcia-Sanz, RamonPerez-Simon, Jose AntonioGomez-Casares, Maria TeresaSanchez-Garcia, JoaquinBarragan, EvaMontesinos, PauOn Behalf Of Pethema Groupacute myeloid leukemiaNext-Generation Sequencingcross-validationsmutational profilegenomic classificationclinical validationSimple Summary Next-Generation Sequencing (NGS) has provided a deeper genetic understanding of acute myeloid leukemia (AML) that has been recently incorporated into AML classification and risk-stratification guidelines. Single molecular analysis has become inefficient and molecular testing based on NGS is emerging as an irreplaceable diagnostic tool in clinical settings. The PETHEMA cooperative group has constituted a nationwide NGS network with centralized analysis in seven high-skilled laboratories. The study of molecular profiles in the "real-life" PETHEMA cohort supports the increasing role of NGS on the clinical management of AML patients. Next-Generation Sequencing (NGS) implementation to perform accurate diagnosis in acute myeloid leukemia (AML) represents a major challenge for molecular laboratories in terms of specialization, standardization, costs and logistical support. In this context, the PETHEMA cooperative group has established the first nationwide diagnostic network of seven reference laboratories to provide standardized NGS studies for AML patients. Cross-validation (CV) rounds are regularly performed to ensure the quality of NGS studies and to keep updated clinically relevant genes recommended for NGS study. The molecular characterization of 2856 samples (1631 derived from the NGS-AML project; NCT03311815) with standardized NGS of consensus genes (ABL1, ASXL1, BRAF, CALR, CBL, CEBPA, CSF3R, DNMT3A, ETV6, EZH2, FLT3, GATA2, HRAS, IDH1, IDH2, JAK2, KIT, KRAS, MPL, NPM1, NRAS, PTPN11, RUNX1, SETBP1, SF3B1, SRSF2, TET2, TP53, U2AF1 and WT1) showed 97% of patients having at least one mutation. The mutational profile was highly variable according to moment of disease, age and sex, and several co-occurring and exclusion relations were detected. Molecular testing based on NGS allowed accurate diagnosis and reliable prognosis stratification of 954 AML patients according to new genomic classification proposed by Tazi et al. Novel molecular subgroups, such as mutated WT1 and mutations in at least two myelodysplasia-related genes, have been associated with an adverse prognosis in our cohort. In this way, the PETHEMA cooperative group efficiently provides an extensive molecular characterization for AML diagnosis and risk stratification, ensuring technical quality and equity in access to NGS studies.MDPI2023info:eu-repo/semantics/articleinfo:eu-repo/semantics/publishedVersionhttps://incliva.portalinvestigacion.com/publicaciones/17130CancersISSN: 20726694reponame:r-INCLIVA. Repositorio Institucional de Producción Científica de INCLIVAinstname:INCLIVAInglésinfo:eu-repo/semantics/openAccessoai:incliva.fundanetsuite.com:p171302026-06-07T16:35:31Z
dc.title.none.fl_str_mv Molecular Landscape and Validation of New Genomic Classification in 2668 Adult AML Patients: Real Life Data from the PETHEMA Registry
title Molecular Landscape and Validation of New Genomic Classification in 2668 Adult AML Patients: Real Life Data from the PETHEMA Registry
spellingShingle Molecular Landscape and Validation of New Genomic Classification in 2668 Adult AML Patients: Real Life Data from the PETHEMA Registry
Sargas, Claudia
acute myeloid leukemia
Next-Generation Sequencing
cross-validations
mutational profile
genomic classification
clinical validation
title_short Molecular Landscape and Validation of New Genomic Classification in 2668 Adult AML Patients: Real Life Data from the PETHEMA Registry
title_full Molecular Landscape and Validation of New Genomic Classification in 2668 Adult AML Patients: Real Life Data from the PETHEMA Registry
title_fullStr Molecular Landscape and Validation of New Genomic Classification in 2668 Adult AML Patients: Real Life Data from the PETHEMA Registry
title_full_unstemmed Molecular Landscape and Validation of New Genomic Classification in 2668 Adult AML Patients: Real Life Data from the PETHEMA Registry
title_sort Molecular Landscape and Validation of New Genomic Classification in 2668 Adult AML Patients: Real Life Data from the PETHEMA Registry
dc.creator.none.fl_str_mv Sargas, Claudia
Ayala, Rosa
Larrayoz, Maria Jose
Chillon, Maria Carmen
Carrillo-Cruz, Estrella
Bilbao-Sieyro, Cristina
Prados de la Torre, Esther
Martinez-Cuadron, David
Rodriguez-Veiga, Rebeca
Boluda, Blanca
Gil, Cristina
Bernal, Teresa
Bergua, Juan Miguel
Algarra, Lorenzo
Tormo, Mar
Martinez-Sanchez, Pilar
Soria, Elena
Serrano, Josefina
Alonso-Dominguez, Juan Manuel
Garcia-Boyero, Raimundo
Amigo, Maria Luz
Herrera-Puente, Pilar
Sayas, Maria Jose
Lavilla-Rubira, Esperanza
Martinez-Lopez, Joaquin
Calasanz, Maria Jose
Garcia-Sanz, Ramon
Perez-Simon, Jose Antonio
Gomez-Casares, Maria Teresa
Sanchez-Garcia, Joaquin
Barragan, Eva
Montesinos, Pau
On Behalf Of Pethema Group
author Sargas, Claudia
author_facet Sargas, Claudia
Ayala, Rosa
Larrayoz, Maria Jose
Chillon, Maria Carmen
Carrillo-Cruz, Estrella
Bilbao-Sieyro, Cristina
Prados de la Torre, Esther
Martinez-Cuadron, David
Rodriguez-Veiga, Rebeca
Boluda, Blanca
Gil, Cristina
Bernal, Teresa
Bergua, Juan Miguel
Algarra, Lorenzo
Tormo, Mar
Martinez-Sanchez, Pilar
Soria, Elena
Serrano, Josefina
Alonso-Dominguez, Juan Manuel
Garcia-Boyero, Raimundo
Amigo, Maria Luz
Herrera-Puente, Pilar
Sayas, Maria Jose
Lavilla-Rubira, Esperanza
Martinez-Lopez, Joaquin
Calasanz, Maria Jose
Garcia-Sanz, Ramon
Perez-Simon, Jose Antonio
Gomez-Casares, Maria Teresa
Sanchez-Garcia, Joaquin
Barragan, Eva
Montesinos, Pau
On Behalf Of Pethema Group
author_role author
author2 Ayala, Rosa
Larrayoz, Maria Jose
Chillon, Maria Carmen
Carrillo-Cruz, Estrella
Bilbao-Sieyro, Cristina
Prados de la Torre, Esther
Martinez-Cuadron, David
Rodriguez-Veiga, Rebeca
Boluda, Blanca
Gil, Cristina
Bernal, Teresa
Bergua, Juan Miguel
Algarra, Lorenzo
Tormo, Mar
Martinez-Sanchez, Pilar
Soria, Elena
Serrano, Josefina
Alonso-Dominguez, Juan Manuel
Garcia-Boyero, Raimundo
Amigo, Maria Luz
Herrera-Puente, Pilar
Sayas, Maria Jose
Lavilla-Rubira, Esperanza
Martinez-Lopez, Joaquin
Calasanz, Maria Jose
Garcia-Sanz, Ramon
Perez-Simon, Jose Antonio
Gomez-Casares, Maria Teresa
Sanchez-Garcia, Joaquin
Barragan, Eva
Montesinos, Pau
On Behalf Of Pethema Group
author2_role author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
dc.subject.none.fl_str_mv acute myeloid leukemia
Next-Generation Sequencing
cross-validations
mutational profile
genomic classification
clinical validation
topic acute myeloid leukemia
Next-Generation Sequencing
cross-validations
mutational profile
genomic classification
clinical validation
description Simple Summary Next-Generation Sequencing (NGS) has provided a deeper genetic understanding of acute myeloid leukemia (AML) that has been recently incorporated into AML classification and risk-stratification guidelines. Single molecular analysis has become inefficient and molecular testing based on NGS is emerging as an irreplaceable diagnostic tool in clinical settings. The PETHEMA cooperative group has constituted a nationwide NGS network with centralized analysis in seven high-skilled laboratories. The study of molecular profiles in the "real-life" PETHEMA cohort supports the increasing role of NGS on the clinical management of AML patients. Next-Generation Sequencing (NGS) implementation to perform accurate diagnosis in acute myeloid leukemia (AML) represents a major challenge for molecular laboratories in terms of specialization, standardization, costs and logistical support. In this context, the PETHEMA cooperative group has established the first nationwide diagnostic network of seven reference laboratories to provide standardized NGS studies for AML patients. Cross-validation (CV) rounds are regularly performed to ensure the quality of NGS studies and to keep updated clinically relevant genes recommended for NGS study. The molecular characterization of 2856 samples (1631 derived from the NGS-AML project; NCT03311815) with standardized NGS of consensus genes (ABL1, ASXL1, BRAF, CALR, CBL, CEBPA, CSF3R, DNMT3A, ETV6, EZH2, FLT3, GATA2, HRAS, IDH1, IDH2, JAK2, KIT, KRAS, MPL, NPM1, NRAS, PTPN11, RUNX1, SETBP1, SF3B1, SRSF2, TET2, TP53, U2AF1 and WT1) showed 97% of patients having at least one mutation. The mutational profile was highly variable according to moment of disease, age and sex, and several co-occurring and exclusion relations were detected. Molecular testing based on NGS allowed accurate diagnosis and reliable prognosis stratification of 954 AML patients according to new genomic classification proposed by Tazi et al. Novel molecular subgroups, such as mutated WT1 and mutations in at least two myelodysplasia-related genes, have been associated with an adverse prognosis in our cohort. In this way, the PETHEMA cooperative group efficiently provides an extensive molecular characterization for AML diagnosis and risk stratification, ensuring technical quality and equity in access to NGS studies.
publishDate 2023
dc.date.none.fl_str_mv 2023
dc.type.none.fl_str_mv info:eu-repo/semantics/article
info:eu-repo/semantics/publishedVersion
format article
status_str publishedVersion
dc.identifier.none.fl_str_mv https://incliva.portalinvestigacion.com/publicaciones/17130
url https://incliva.portalinvestigacion.com/publicaciones/17130
dc.language.none.fl_str_mv Inglés
language_invalid_str_mv Inglés
dc.rights.none.fl_str_mv info:eu-repo/semantics/openAccess
eu_rights_str_mv openAccess
dc.publisher.none.fl_str_mv MDPI
publisher.none.fl_str_mv MDPI
dc.source.none.fl_str_mv Cancers
ISSN: 20726694
reponame:r-INCLIVA. Repositorio Institucional de Producción Científica de INCLIVA
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instname_str INCLIVA
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