Mutation in Chek2 triggers von Hippel-Lindau hemangioblastoma growth

Purpose: Von Hippel-Lindau (VHL) is a rare inherited disease mainly characterized by the growth of tumours, predominantly hemangioblastomas (Hbs) in the CNS and retina, and renal carcinomas. The natural history of VHL disease is variable, differing in the age of onset and its penetrance, even among...

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Detalles Bibliográficos
Autores: Cabrera-Montes, Jorge, Aguirre, Daniel T., Viñas-López, Jesús, Lorente-Herraiz, Laura, Recio-Poveda, Lucía, Albiñana, Virginia, Pérez Pérez, Julián, Botella, Luisa María, Cuesta, Ángel M.
Tipo de recurso: artículo
Estado:Versión publicada
Fecha de publicación:2023
País:España
Institución:Consejo Superior de Investigaciones Científicas (CSIC)
Repositorio:DIGITAL.CSIC. Repositorio Institucional del CSIC
OAI Identifier:oai:digital.csic.es:10261/337265
Acceso en línea:http://hdl.handle.net/10261/337265
Access Level:acceso abierto
Palabra clave:CNS Hemangioblastomas
Chek2
Personalized medicine
Rare cancer
ccRCC
von Hippel-Lindau disease (VHL)
Descripción
Sumario:Purpose: Von Hippel-Lindau (VHL) is a rare inherited disease mainly characterized by the growth of tumours, predominantly hemangioblastomas (Hbs) in the CNS and retina, and renal carcinomas. The natural history of VHL disease is variable, differing in the age of onset and its penetrance, even among relatives. Unfortunately, sometimes VHL shows more severe than average: the onset starts in adolescence, and surgeries are required almost every year. In these cases, the factor that triggers the appearance and growth of Hbs usually remains unknown, although additional mutations are suspected.