Hirschsprung disease with debut in adult age as acute intestinal obstruction: case report

Hirschsprung’s disease is characterized by absence of ganglion cells in submucosal and myenteric plexus of distal bowel. Most cases become manifest during the neonatal period, but in rare instances, this disease is initially diagnosed in adult age. It usually presents as severe constipation with col...

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Detalles Bibliográficos
Autores: López Ruiz, José Antonio, Tallón Aguilar, Luis, Sánchez Moreno, Laura, López Pérez, José, Pareja Ciuró, Felipe, Oliva Mompean, Fernando, Padillo Ruiz, Francisco Javier
Tipo de recurso: artículo
Estado:Versión publicada
Fecha de publicación:2016
País:España
Institución:Universidad de Sevilla (US)
Repositorio:idUS. Depósito de Investigación de la Universidad de Sevilla
OAI Identifier:oai:idus.us.es:11441/158887
Acceso en línea:https://hdl.handle.net/11441/158887
https://doi.org/10.17235/reed.2016.3841/2015
Access Level:acceso abierto
Palabra clave:Hirschsprung disease
Megacolon
Intestinal obstruction
Descripción
Sumario:Hirschsprung’s disease is characterized by absence of ganglion cells in submucosal and myenteric plexus of distal bowel. Most cases become manifest during the neonatal period, but in rare instances, this disease is initially diagnosed in adult age. It usually presents as severe constipation with colonic dilatation proximal to the agangli onic segment. The treatment is surgical, removing the aganglionic segment and restoring continuity of digestive tract. The disease rarely presents as an acute intestinal obstruction. We report a case not previously diagnosed, which presented as a massive colonic dilatation with a maximum diameter of 44 cm, with imminent risk of drilling that forced to perform an emergency surgery. We include a review of existing literature.