HMGA1 regulates trabectedin sensitivity in advanced soft-tissue sarcoma (STS)

HMGA1 is a structural epigenetic chromatin factor that has been associated with tumor progression and drug resistance. Here, we reported the prognostic/predictive value of HMGA1 for trabectedin in advanced soft-tissue sarcoma (STS) and the effect of inhibiting HMGA1 or the mTOR downstream pathway in...

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Autores: Moura, David S., Mondaza-Hernandez, Jose L., Sanchez-Bustos, Paloma, Peña-Chilet, Maria, Cordero-Varela, Juan A., Lopez-Alvarez, Maria, Carrillo-Garcia, Jaime, Martin-Ruiz, Marta, Romero-Gonzalez, Pablo, Renshaw-Calderon, Marta, Ramos, Rafel|||0000-0001-7970-5537, Marcilla, David, Alvarez-Alegret, Ramiro, Agra Pujol, Carolina|||0000-0003-4843-5786, Izquierdo, Francisco, Ortega-Medina, Luis, Martin-Davila, Francisco, Hernandez-Leon, Carmen Nieves, Romagosa Perez Portabella, Maria Cleofe|||0000-0002-9478-7320, Salgado, Maria Angeles Vaz, Lavernia, Javier, Bagué Rosell, Sílvia|||0000-0001-9980-7231, Mayodormo-Aranda, Empar, Alvarez, Rosa|||0000-0003-0935-8298, Valverde Morales, Claudia Maria, Martínez Trufero, Javier|||0000-0002-0997-2573, Castilla-Ramirez, Carolina, Gutiérrez, Antonio|||0000-0001-9062-077X, Dopazo, Joaquín|||0000-0003-3318-120X, Hindi, Nadia|||0000-0002-5864-762X, Garcia-Foncillas, Jesus, Martín-Broto, Javier|||0000-0001-7350-6916
Tipo de recurso: artículo
Fecha de publicación:2024
País:España
Institución:Universitat Autònoma de Barcelona
Repositorio:Dipòsit Digital de Documents de la UAB
Idioma:inglés
OAI Identifier:oai:ddd.uab.cat:292716
Acceso en línea:https://ddd.uab.cat/record/292716
https://dx.doi.org/urn:doi:10.1007/s00018-024-05250-y
Access Level:acceso abierto
Palabra clave:HMGA1
Leiomyosarcoma
Mtor pathway
Soft-tissue sarcoma
Trabectedin
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spelling HMGA1 regulates trabectedin sensitivity in advanced soft-tissue sarcoma (STS)A Spanish Group for Research on Sarcomas (GEIS) studyMoura, David S.Mondaza-Hernandez, Jose L.Sanchez-Bustos, PalomaPeña-Chilet, MariaCordero-Varela, Juan A.Lopez-Alvarez, MariaCarrillo-Garcia, JaimeMartin-Ruiz, MartaRomero-Gonzalez, PabloRenshaw-Calderon, MartaRamos, Rafel|||0000-0001-7970-5537Marcilla, DavidAlvarez-Alegret, RamiroAgra Pujol, Carolina|||0000-0003-4843-5786Izquierdo, FranciscoOrtega-Medina, LuisMartin-Davila, FranciscoHernandez-Leon, Carmen NievesRomagosa Perez Portabella, Maria Cleofe|||0000-0002-9478-7320Salgado, Maria Angeles VazLavernia, JavierBagué Rosell, Sílvia|||0000-0001-9980-7231Mayodormo-Aranda, EmparAlvarez, Rosa|||0000-0003-0935-8298Valverde Morales, Claudia MariaMartínez Trufero, Javier|||0000-0002-0997-2573Castilla-Ramirez, CarolinaGutiérrez, Antonio|||0000-0001-9062-077XDopazo, Joaquín|||0000-0003-3318-120XHindi, Nadia|||0000-0002-5864-762XGarcia-Foncillas, JesusMartín-Broto, Javier|||0000-0001-7350-6916HMGA1LeiomyosarcomaMtor pathwaySoft-tissue sarcomaTrabectedinHMGA1 is a structural epigenetic chromatin factor that has been associated with tumor progression and drug resistance. Here, we reported the prognostic/predictive value of HMGA1 for trabectedin in advanced soft-tissue sarcoma (STS) and the effect of inhibiting HMGA1 or the mTOR downstream pathway in trabectedin activity. The prognostic/predictive value of HMGA1 expression was assessed in a cohort of 301 STS patients at mRNA (n = 133) and protein level (n = 272), by HTG EdgeSeq transcriptomics and immunohistochemistry, respectively. The effect of HMGA1 silencing on trabectedin activity and gene expression profiling was measured in leiomyosarcoma cells. The effect of combining mTOR inhibitors with trabectedin was assessed on cell viability in vitro studies, whereas in vivo studies tested the activity of this combination. HMGA1 mRNA and protein expression were significantly associated with worse progression-free survival of trabectedin and worse overall survival in STS. HMGA1 silencing sensitized leiomyosarcoma cells for trabectedin treatment, reducing the spheroid area and increasing cell death. The downregulation of HGMA1 significantly decreased the enrichment of some specific gene sets, including the PI3K/AKT/mTOR pathway. The inhibition of mTOR, sensitized leiomyosarcoma cultures for trabectedin treatment, increasing cell death. In in vivo studies, the combination of rapamycin with trabectedin downregulated HMGA1 expression and stabilized tumor growth of 3-methylcholantrene-induced sarcoma-like models. HMGA1 is an adverse prognostic factor for trabectedin treatment in advanced STS. HMGA1 silencing increases trabectedin efficacy, in part by modulating the mTOR signaling pathway. Trabectedin plus mTOR inhibitors are active in preclinical models of sarcoma, downregulating HMGA1 expression levels and stabilizing tumor growth.Universitat Autònoma de Barcelona. Departament de Ciències Morfològiques 22024-01-0120242024-01-01Articlehttp://purl.org/coar/resource_type/c_6501VoRhttp://purl.org/coar/version/c_970fb48d4fbd8a85info:eu-repo/semantics/articleapplication/pdfhttps://ddd.uab.cat/record/292716https://dx.doi.org/urn:doi:10.1007/s00018-024-05250-yreponame:Dipòsit Digital de Documents de la UABinstname:Universitat Autònoma de BarcelonaInglésengEuropean Commission https://doi.org/10.13039/501100000780 825806open accesshttp://purl.org/coar/access_right/c_abf2Aquest document està subjecte a una llicència d'ús Creative Commons. Es permet la reproducció total o parcial, la distribució, la comunicació pública de l'obra i la creació d'obres derivades, fins i tot amb finalitats comercials, sempre i quan es reconegui l'autoria de l'obra original.https://creativecommons.org/licenses/by/4.0/info:eu-repo/semantics/openAccessoai:ddd.uab.cat:2927162026-06-06T12:50:31Z
dc.title.none.fl_str_mv HMGA1 regulates trabectedin sensitivity in advanced soft-tissue sarcoma (STS)
A Spanish Group for Research on Sarcomas (GEIS) study
title HMGA1 regulates trabectedin sensitivity in advanced soft-tissue sarcoma (STS)
spellingShingle HMGA1 regulates trabectedin sensitivity in advanced soft-tissue sarcoma (STS)
Moura, David S.
HMGA1
Leiomyosarcoma
Mtor pathway
Soft-tissue sarcoma
Trabectedin
title_short HMGA1 regulates trabectedin sensitivity in advanced soft-tissue sarcoma (STS)
title_full HMGA1 regulates trabectedin sensitivity in advanced soft-tissue sarcoma (STS)
title_fullStr HMGA1 regulates trabectedin sensitivity in advanced soft-tissue sarcoma (STS)
title_full_unstemmed HMGA1 regulates trabectedin sensitivity in advanced soft-tissue sarcoma (STS)
title_sort HMGA1 regulates trabectedin sensitivity in advanced soft-tissue sarcoma (STS)
dc.creator.none.fl_str_mv Moura, David S.
Mondaza-Hernandez, Jose L.
Sanchez-Bustos, Paloma
Peña-Chilet, Maria
Cordero-Varela, Juan A.
Lopez-Alvarez, Maria
Carrillo-Garcia, Jaime
Martin-Ruiz, Marta
Romero-Gonzalez, Pablo
Renshaw-Calderon, Marta
Ramos, Rafel|||0000-0001-7970-5537
Marcilla, David
Alvarez-Alegret, Ramiro
Agra Pujol, Carolina|||0000-0003-4843-5786
Izquierdo, Francisco
Ortega-Medina, Luis
Martin-Davila, Francisco
Hernandez-Leon, Carmen Nieves
Romagosa Perez Portabella, Maria Cleofe|||0000-0002-9478-7320
Salgado, Maria Angeles Vaz
Lavernia, Javier
Bagué Rosell, Sílvia|||0000-0001-9980-7231
Mayodormo-Aranda, Empar
Alvarez, Rosa|||0000-0003-0935-8298
Valverde Morales, Claudia Maria
Martínez Trufero, Javier|||0000-0002-0997-2573
Castilla-Ramirez, Carolina
Gutiérrez, Antonio|||0000-0001-9062-077X
Dopazo, Joaquín|||0000-0003-3318-120X
Hindi, Nadia|||0000-0002-5864-762X
Garcia-Foncillas, Jesus
Martín-Broto, Javier|||0000-0001-7350-6916
author Moura, David S.
author_facet Moura, David S.
Mondaza-Hernandez, Jose L.
Sanchez-Bustos, Paloma
Peña-Chilet, Maria
Cordero-Varela, Juan A.
Lopez-Alvarez, Maria
Carrillo-Garcia, Jaime
Martin-Ruiz, Marta
Romero-Gonzalez, Pablo
Renshaw-Calderon, Marta
Ramos, Rafel|||0000-0001-7970-5537
Marcilla, David
Alvarez-Alegret, Ramiro
Agra Pujol, Carolina|||0000-0003-4843-5786
Izquierdo, Francisco
Ortega-Medina, Luis
Martin-Davila, Francisco
Hernandez-Leon, Carmen Nieves
Romagosa Perez Portabella, Maria Cleofe|||0000-0002-9478-7320
Salgado, Maria Angeles Vaz
Lavernia, Javier
Bagué Rosell, Sílvia|||0000-0001-9980-7231
Mayodormo-Aranda, Empar
Alvarez, Rosa|||0000-0003-0935-8298
Valverde Morales, Claudia Maria
Martínez Trufero, Javier|||0000-0002-0997-2573
Castilla-Ramirez, Carolina
Gutiérrez, Antonio|||0000-0001-9062-077X
Dopazo, Joaquín|||0000-0003-3318-120X
Hindi, Nadia|||0000-0002-5864-762X
Garcia-Foncillas, Jesus
Martín-Broto, Javier|||0000-0001-7350-6916
author_role author
author2 Mondaza-Hernandez, Jose L.
Sanchez-Bustos, Paloma
Peña-Chilet, Maria
Cordero-Varela, Juan A.
Lopez-Alvarez, Maria
Carrillo-Garcia, Jaime
Martin-Ruiz, Marta
Romero-Gonzalez, Pablo
Renshaw-Calderon, Marta
Ramos, Rafel|||0000-0001-7970-5537
Marcilla, David
Alvarez-Alegret, Ramiro
Agra Pujol, Carolina|||0000-0003-4843-5786
Izquierdo, Francisco
Ortega-Medina, Luis
Martin-Davila, Francisco
Hernandez-Leon, Carmen Nieves
Romagosa Perez Portabella, Maria Cleofe|||0000-0002-9478-7320
Salgado, Maria Angeles Vaz
Lavernia, Javier
Bagué Rosell, Sílvia|||0000-0001-9980-7231
Mayodormo-Aranda, Empar
Alvarez, Rosa|||0000-0003-0935-8298
Valverde Morales, Claudia Maria
Martínez Trufero, Javier|||0000-0002-0997-2573
Castilla-Ramirez, Carolina
Gutiérrez, Antonio|||0000-0001-9062-077X
Dopazo, Joaquín|||0000-0003-3318-120X
Hindi, Nadia|||0000-0002-5864-762X
Garcia-Foncillas, Jesus
Martín-Broto, Javier|||0000-0001-7350-6916
author2_role author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
dc.contributor.none.fl_str_mv Universitat Autònoma de Barcelona. Departament de Ciències Morfològiques
dc.subject.none.fl_str_mv HMGA1
Leiomyosarcoma
Mtor pathway
Soft-tissue sarcoma
Trabectedin
topic HMGA1
Leiomyosarcoma
Mtor pathway
Soft-tissue sarcoma
Trabectedin
description HMGA1 is a structural epigenetic chromatin factor that has been associated with tumor progression and drug resistance. Here, we reported the prognostic/predictive value of HMGA1 for trabectedin in advanced soft-tissue sarcoma (STS) and the effect of inhibiting HMGA1 or the mTOR downstream pathway in trabectedin activity. The prognostic/predictive value of HMGA1 expression was assessed in a cohort of 301 STS patients at mRNA (n = 133) and protein level (n = 272), by HTG EdgeSeq transcriptomics and immunohistochemistry, respectively. The effect of HMGA1 silencing on trabectedin activity and gene expression profiling was measured in leiomyosarcoma cells. The effect of combining mTOR inhibitors with trabectedin was assessed on cell viability in vitro studies, whereas in vivo studies tested the activity of this combination. HMGA1 mRNA and protein expression were significantly associated with worse progression-free survival of trabectedin and worse overall survival in STS. HMGA1 silencing sensitized leiomyosarcoma cells for trabectedin treatment, reducing the spheroid area and increasing cell death. The downregulation of HGMA1 significantly decreased the enrichment of some specific gene sets, including the PI3K/AKT/mTOR pathway. The inhibition of mTOR, sensitized leiomyosarcoma cultures for trabectedin treatment, increasing cell death. In in vivo studies, the combination of rapamycin with trabectedin downregulated HMGA1 expression and stabilized tumor growth of 3-methylcholantrene-induced sarcoma-like models. HMGA1 is an adverse prognostic factor for trabectedin treatment in advanced STS. HMGA1 silencing increases trabectedin efficacy, in part by modulating the mTOR signaling pathway. Trabectedin plus mTOR inhibitors are active in preclinical models of sarcoma, downregulating HMGA1 expression levels and stabilizing tumor growth.
publishDate 2024
dc.date.none.fl_str_mv 2
2024-01-01
2024
2024-01-01
dc.type.none.fl_str_mv Article
http://purl.org/coar/resource_type/c_6501
VoR
http://purl.org/coar/version/c_970fb48d4fbd8a85
dc.type.openaire.fl_str_mv info:eu-repo/semantics/article
format article
dc.identifier.none.fl_str_mv https://ddd.uab.cat/record/292716
https://dx.doi.org/urn:doi:10.1007/s00018-024-05250-y
url https://ddd.uab.cat/record/292716
https://dx.doi.org/urn:doi:10.1007/s00018-024-05250-y
dc.language.none.fl_str_mv Inglés
eng
language_invalid_str_mv Inglés
language eng
dc.relation.none.fl_str_mv European Commission https://doi.org/10.13039/501100000780 825806
dc.rights.none.fl_str_mv open access
http://purl.org/coar/access_right/c_abf2
https://creativecommons.org/licenses/by/4.0/
dc.rights.openaire.fl_str_mv info:eu-repo/semantics/openAccess
rights_invalid_str_mv open access
http://purl.org/coar/access_right/c_abf2
https://creativecommons.org/licenses/by/4.0/
eu_rights_str_mv openAccess
dc.format.none.fl_str_mv application/pdf
dc.source.none.fl_str_mv reponame:Dipòsit Digital de Documents de la UAB
instname:Universitat Autònoma de Barcelona
instname_str Universitat Autònoma de Barcelona
reponame_str Dipòsit Digital de Documents de la UAB
collection Dipòsit Digital de Documents de la UAB
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repository.mail.fl_str_mv
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