Safety and Efficacy of the Use of pdVWF/FVIII-C in Patients with von Willebrand Disease

Introduction: Plasma-derived von Willebrand factor containing FVIII concentrates (pdVWF/FVIII-C) are indicated as replacement therapy for patients with von Willebrand disease (VWD). This study assessed safety and efficacy associated with long-term real-world experience of the pdVWF/FVIII-C, Fanhdi,...

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Autores: Benítez Hidalgo, Olga|||0000-0002-2883-9049, Marzo Alonso, Cristina, López Jaime, Francisco José, Carrasco Exposito, Marina|||0000-0001-8301-8000, Nieto Hernández, Maria del Mar, Afonso, Natalia, Lei, Alejhandra, Whyms, Dermot, Hanna, Kim, Aragonés, Maria Esperança, Torres, Mireia, Oliveras, Juan
Tipo de recurso: artículo
Fecha de publicación:2025
País:España
Institución:Universitat Autònoma de Barcelona
Repositorio:Dipòsit Digital de Documents de la UAB
Idioma:inglés
OAI Identifier:oai:ddd.uab.cat:320040
Acceso en línea:https://ddd.uab.cat/record/320040
https://dx.doi.org/urn:doi:10.1177/10760296251327593
Access Level:acceso abierto
Palabra clave:Bleeding
Invasive procedures
On-demand treatment
Plasma-derived von Willebrand factor/factor VIII concentrate
Prophylaxis treatment
Real world evidence
Surgery
Von Willebrand disease
Descripción
Sumario:Introduction: Plasma-derived von Willebrand factor containing FVIII concentrates (pdVWF/FVIII-C) are indicated as replacement therapy for patients with von Willebrand disease (VWD). This study assessed safety and efficacy associated with long-term real-world experience of the pdVWF/FVIII-C, Fanhdi, in patients with VWD. Methods: This observational, prospective, post-authorization cohort study was conducted at five centers in Spain. Patients with VWD were treated with the pdVWF/FVIII-C to achieve satisfactory hemostasis for on-demand (bleeding episodes and surgical/invasive procedures) and prophylaxis treatment. Clinical efficacy was evaluated as the response to treatment in both settings. Safety parameters were assessed. Results: Fifteen VWD patients received at least one dose of the pdVWF/FVIII-C and were followed for 12 months. Forty-six bleeding episodes were reported for 9 (60.0%) patients, and 6 surgical/invasive procedures for 5 (33.3%) patients. Most frequently reported bleedings were gastrointestinal (3 [33.0%] patients) and gynecological (3 [33.0%] patients). No complications nor bleeding episodes related to surgical/invasive procedures were reported. Overall clinical efficacy of treatment (including on-demand and prophylaxis) achieved 100% excellent and/or good (n = 15 patients), being excellent for 7 (46.7%) patients. There were 27 treatment-emergent adverse events in 8 (53.3%) patients, 11 serious adverse events in 3 (20.0%) patients, but none of them were drug-related. No clinical signs and symptoms of immunogenicity or thromboembolic events were reported. Conclusions: This real-world evidence study confirmed the efficacy of the pdVWF/FVIII-C as on-demand and/or prophylaxis treatment in patients with bleeding episodes or surgical procedures in VWD. Fanhdi was well tolerated without any safety concerns.