Dual loss of the SWI/SNF complex ATPases SMARCA4/BRG1 and SMARCA2/BRM is highly sensitive and specific for small cell carcinoma of the ovary, hypercalcaemic type

Small cell carcinoma of the ovary, hypercalcaemic type () is a lethal and sometimes familial ovarian tumour of young women and children. We and others recently discovered that over 90% of harbour inactivating mutations in the chromatin remodelling gene with concomitant loss of its encoded protein ()...

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Detalles Bibliográficos
Autores: Karnezis, Anthony N., Wang, Yemin, Ramos, Pilar, Hendricks, William P. D., Oliva, Esther, D'Angelo, Emanuela|||0000-0002-6173-1806, Prat, Jaime|||0000-0002-9787-3304, Nucci, Marisa R., Nielsen, Torsten O., Chow, Christine, Leung, Samuel, Kommoss, Friedrich, Kommoss, Stefan, Silva, Annacarolina, Ronnett, Brigitte M., Rabban, Joseph T., Bowtell, David D., Weissman, Bernard E., Trent, Jeffrey M., Gilks, C. Blake, Huntsman, David G.|||0000-0003-4934-3322
Tipo de recurso: artículo
Fecha de publicación:2015
País:España
Institución:Universitat Autònoma de Barcelona
Repositorio:Dipòsit Digital de Documents de la UAB
Idioma:inglés
OAI Identifier:oai:ddd.uab.cat:185416
Acceso en línea:https://ddd.uab.cat/record/185416
https://dx.doi.org/urn:doi:10.1002/path.4633
Access Level:acceso abierto
Palabra clave:Small cell carcinoma
Hypercalcaemic type
Rhabdoid tumour
SMARCA4/BRG1
SMARCA2/BRM
SMARCB1/INI1
SWI/SNF
HDAC inhibitor
Inhibitor
Trichostatin A
Epigenetic silencing
Descripción
Sumario:Small cell carcinoma of the ovary, hypercalcaemic type () is a lethal and sometimes familial ovarian tumour of young women and children. We and others recently discovered that over 90% of harbour inactivating mutations in the chromatin remodelling gene with concomitant loss of its encoded protein (), one of two mutually exclusive of the / chromatin remodelling complex. To determine the specificity of loss for , we examined the expression of by immunohistochemistry in more than 3000 primary gynaecological tumours. Among ovarian tumours, it was only absent in clear cell carcinoma (15 of 360, 4%). In the uterus, it was absent in endometrial stromal sarcomas (4 of 52, 8%) and high-grade endometrioid carcinomas (2 of 338, 1%). Recent studies have shown that (), the other mutually exclusive of the / complex, is necessary for survival of tumour cells lacking . Therefore, we examined expression and discovered that all -negative also lacked protein by , including the cell lines and . Among ovarian tumours, the / dual loss phenotype appears completely specific for . loss was not due to mutation but rather from an absence of expression, which was restored by treatment with the histone deacetylase inhibitor trichostatin A. Re-expression of or inhibited the growth of and cell lines. Our results indicate that loss, either alone or with , is highly sensitive and specific for and that restoration of either / can inhibit the growth of cell lines. © 2015 The Authors. The Journal of Pathology published by John Wiley & Sons Ltd on behalf of Pathological Society of Great Britain and Ireland.