Dysfunctional Homozygous VRK1-D263G Variant Impairs the Assembly of Cajal Bodies and DNA Damage Response in Hereditary Spastic Paraplegia

[Background and Objectives]: To conduct a genetic and molecular functional study of a family with members affected of hereditary spastic paraplegia (HSP) of unknown origin and carrying a novel pathogenic vaccinia-related kinase 1 (VRK1) variant.

Detalles Bibliográficos
Autores: Morejón-García, Patricia, Keren, Boris, Marcos-Alcalde, Íñigo, Gómez-Puertas, Paulino, Mochel, Fanny, Lazo, Pedro A.
Tipo de recurso: artículo
Estado:Versión publicada
Fecha de publicación:2021
País:España
Institución:Consejo Superior de Investigaciones Científicas (CSIC)
Repositorio:DIGITAL.CSIC. Repositorio Institucional del CSIC
OAI Identifier:oai:digital.csic.es:10261/261383
Acceso en línea:http://hdl.handle.net/10261/261383
Access Level:acceso abierto
Palabra clave:All Neuromuscular Disease
All Genetics
Developmental disorders
Spastic paraplegia
Descripción
Sumario:[Background and Objectives]: To conduct a genetic and molecular functional study of a family with members affected of hereditary spastic paraplegia (HSP) of unknown origin and carrying a novel pathogenic vaccinia-related kinase 1 (VRK1) variant.