Development of pathogenicity predictors specific for variants that do not comply with clinical guidelines for the use of computational evidence

[Background] Strict guidelines delimit the use of computational information in the clinical setting, due to the still moderate accuracy of in silico tools. These guidelines indicate that several tools should always be used and that full coincidence between them is required if we want to consider the...

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Detalles Bibliográficos
Autores: Álvarez de la Campa, Elena, Padilla, Natàlia, Cruz, Xavier de la
Tipo de recurso: artículo
Estado:Versión publicada
Fecha de publicación:2017
País:España
Institución:Consejo Superior de Investigaciones Científicas (CSIC)
Repositorio:DIGITAL.CSIC. Repositorio Institucional del CSIC
OAI Identifier:oai:digital.csic.es:10261/174264
Acceso en línea:http://hdl.handle.net/10261/174264
Access Level:acceso abierto
Palabra clave:In silico pathogenicity predictors
Protein sequence variants
Molecular diagnostics
Missense variants
Next-generation sequencing
Descripción
Sumario:[Background] Strict guidelines delimit the use of computational information in the clinical setting, due to the still moderate accuracy of in silico tools. These guidelines indicate that several tools should always be used and that full coincidence between them is required if we want to consider their results as supporting evidence in medical decision processes. Application of this simple rule certainly decreases the error rate of in silico pathogenicity assignments. However, when predictors disagree this rule results in the rejection of potentially valuable information for a number of variants. In this work, we focus on these variants of the protein sequence and develop specific predictors to help improve the success rate of their annotation.