Kidins220 sets the threshold for survival of neural stem cells and progenitors to sustain adult neurogenesis

In the adult mammalian brain, neural stem cells (NSCs) located in highly restricted niches sustain the generation of new neurons that integrate into existing circuits. A reduction in adult neurogenesis is linked to ageing and neurodegeneration, whereas dysregulation of proliferation and survival of...

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Autores: del Puerto, Ana, López Fonseca, Coral, Simón-García, Ana, Martí-Prado, Beatriz, Barrios Muñoz, Ana Laura, Pose-Utrilla, Julia, López-Menéndez, Celia, Alcover-Sanchez, Berta, Cesca, Fabrizia, Schiavo, Giampietro, Campanero, Miguel R., Fariñas, Isabel, Iglesias, Teresa, Porlán Alonso, Eva
Tipo de recurso: artículo
Fecha de publicación:2023
País:España
Institución:Universidad Autónoma de Madrid
Repositorio:Biblos-e Archivo. Repositorio Institucional de la UAM
Idioma:inglés
OAI Identifier:oai:repositorio.uam.es:10486/712194
Acceso en línea:http://hdl.handle.net/10486/712194
https://dx.doi.org/10.1038/s41419-023-05995-7
Access Level:acceso abierto
Palabra clave:Adult
adult stem cells
animals
epidermal growth factor
glycogen synthase kinase 3
hippocampus
humans
mammals
mice
neural stem cells
neurogenesis
neurons
Biología y Biomedicina / Biología
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oai_identifier_str oai:repositorio.uam.es:10486/712194
network_acronym_str ES
network_name_str España
repository_id_str
dc.title.none.fl_str_mv Kidins220 sets the threshold for survival of neural stem cells and progenitors to sustain adult neurogenesis
title Kidins220 sets the threshold for survival of neural stem cells and progenitors to sustain adult neurogenesis
spellingShingle Kidins220 sets the threshold for survival of neural stem cells and progenitors to sustain adult neurogenesis
del Puerto, Ana
Adult
adult stem cells
animals
epidermal growth factor
glycogen synthase kinase 3
hippocampus
humans
mammals
mice
neural stem cells
neurogenesis
neurons
Biología y Biomedicina / Biología
title_short Kidins220 sets the threshold for survival of neural stem cells and progenitors to sustain adult neurogenesis
title_full Kidins220 sets the threshold for survival of neural stem cells and progenitors to sustain adult neurogenesis
title_fullStr Kidins220 sets the threshold for survival of neural stem cells and progenitors to sustain adult neurogenesis
title_full_unstemmed Kidins220 sets the threshold for survival of neural stem cells and progenitors to sustain adult neurogenesis
title_sort Kidins220 sets the threshold for survival of neural stem cells and progenitors to sustain adult neurogenesis
dc.creator.none.fl_str_mv del Puerto, Ana
López Fonseca, Coral
Simón-García, Ana
Martí-Prado, Beatriz
Barrios Muñoz, Ana Laura
Pose-Utrilla, Julia
López-Menéndez, Celia
Alcover-Sanchez, Berta
Cesca, Fabrizia
Schiavo, Giampietro
Campanero, Miguel R.
Fariñas, Isabel
Iglesias, Teresa
Porlán Alonso, Eva
author del Puerto, Ana
author_facet del Puerto, Ana
López Fonseca, Coral
Simón-García, Ana
Martí-Prado, Beatriz
Barrios Muñoz, Ana Laura
Pose-Utrilla, Julia
López-Menéndez, Celia
Alcover-Sanchez, Berta
Cesca, Fabrizia
Schiavo, Giampietro
Campanero, Miguel R.
Fariñas, Isabel
Iglesias, Teresa
Porlán Alonso, Eva
author_role author
author2 López Fonseca, Coral
Simón-García, Ana
Martí-Prado, Beatriz
Barrios Muñoz, Ana Laura
Pose-Utrilla, Julia
López-Menéndez, Celia
Alcover-Sanchez, Berta
Cesca, Fabrizia
Schiavo, Giampietro
Campanero, Miguel R.
Fariñas, Isabel
Iglesias, Teresa
Porlán Alonso, Eva
author2_role author
author
author
author
author
author
author
author
author
author
author
author
author
dc.contributor.none.fl_str_mv Departamento de Biología Molecular
Facultad de Ciencias
dc.subject.none.fl_str_mv Adult
adult stem cells
animals
epidermal growth factor
glycogen synthase kinase 3
hippocampus
humans
mammals
mice
neural stem cells
neurogenesis
neurons
Biología y Biomedicina / Biología
topic Adult
adult stem cells
animals
epidermal growth factor
glycogen synthase kinase 3
hippocampus
humans
mammals
mice
neural stem cells
neurogenesis
neurons
Biología y Biomedicina / Biología
description In the adult mammalian brain, neural stem cells (NSCs) located in highly restricted niches sustain the generation of new neurons that integrate into existing circuits. A reduction in adult neurogenesis is linked to ageing and neurodegeneration, whereas dysregulation of proliferation and survival of NSCs have been hypothesized to be at the origin of glioma. Thus, unravelling the molecular underpinnings of the regulated activation that NSCs must undergo to proliferate and generate new progeny is of considerable relevance. Current research has identified cues promoting or restraining NSCs activation. Yet, whether NSCs depend on external signals to survive or if intrinsic factors establish a threshold for sustaining their viability remains elusive, even if this knowledge could involve potential for devising novel therapeutic strategies. Kidins220 (Kinase D-interacting substrate of 220 kDa) is an essential effector of crucial pathways for neuronal survival and differentiation. It is dramatically altered in cancer and in neurological and neurodegenerative disorders, emerging as a regulatory molecule with important functions in human disease. Herein, we discover severe neurogenic deficits and hippocampal-based spatial memory defects accompanied by increased neuroblast death and high loss of newly formed neurons in Kidins220 deficient mice. Mechanistically, we demonstrate that Kidins220-dependent activation of AKT in response to EGF restraints GSK3 activity preventing NSCs apoptosis. We also show that NSCs with Kidins220 can survive with lower concentrations of EGF than the ones lacking this molecule. Hence, Kidins220 levels set a molecular threshold for survival in response to mitogens, allowing adult NSCs growth and expansion. Our study identifies Kidins220 as a key player for sensing the availability of growth factors to sustain adult neurogenesis, uncovering a molecular link that may help paving the way towards neurorepair
publishDate 2023
dc.date.none.fl_str_mv 2023
2023-08-01
dc.type.none.fl_str_mv research article
http://purl.org/coar/resource_type/c_2df8fbb1
VoR
http://purl.org/coar/version/c_970fb48d4fbd8a85
dc.type.openaire.fl_str_mv info:eu-repo/semantics/article
format article
dc.identifier.none.fl_str_mv http://hdl.handle.net/10486/712194
https://dx.doi.org/10.1038/s41419-023-05995-7
url http://hdl.handle.net/10486/712194
https://dx.doi.org/10.1038/s41419-023-05995-7
dc.language.none.fl_str_mv Inglés
eng
language_invalid_str_mv Inglés
language eng
dc.rights.none.fl_str_mv open access
http://purl.org/coar/access_right/c_abf2
dc.rights.openaire.fl_str_mv info:eu-repo/semantics/openAccess
rights_invalid_str_mv open access
http://purl.org/coar/access_right/c_abf2
eu_rights_str_mv openAccess
dc.format.none.fl_str_mv application/pdf
dc.publisher.none.fl_str_mv Springer Nature
publisher.none.fl_str_mv Springer Nature
dc.source.none.fl_str_mv reponame:Biblos-e Archivo. Repositorio Institucional de la UAM
instname:Universidad Autónoma de Madrid
instname_str Universidad Autónoma de Madrid
reponame_str Biblos-e Archivo. Repositorio Institucional de la UAM
collection Biblos-e Archivo. Repositorio Institucional de la UAM
repository.name.fl_str_mv
repository.mail.fl_str_mv
_version_ 1869409414768754688
spelling Kidins220 sets the threshold for survival of neural stem cells and progenitors to sustain adult neurogenesisdel Puerto, AnaLópez Fonseca, CoralSimón-García, AnaMartí-Prado, BeatrizBarrios Muñoz, Ana LauraPose-Utrilla, JuliaLópez-Menéndez, CeliaAlcover-Sanchez, BertaCesca, FabriziaSchiavo, GiampietroCampanero, Miguel R.Fariñas, IsabelIglesias, TeresaPorlán Alonso, EvaAdultadult stem cellsanimalsepidermal growth factorglycogen synthase kinase 3hippocampushumansmammalsmiceneural stem cellsneurogenesisneuronsBiología y Biomedicina / BiologíaIn the adult mammalian brain, neural stem cells (NSCs) located in highly restricted niches sustain the generation of new neurons that integrate into existing circuits. A reduction in adult neurogenesis is linked to ageing and neurodegeneration, whereas dysregulation of proliferation and survival of NSCs have been hypothesized to be at the origin of glioma. Thus, unravelling the molecular underpinnings of the regulated activation that NSCs must undergo to proliferate and generate new progeny is of considerable relevance. Current research has identified cues promoting or restraining NSCs activation. Yet, whether NSCs depend on external signals to survive or if intrinsic factors establish a threshold for sustaining their viability remains elusive, even if this knowledge could involve potential for devising novel therapeutic strategies. Kidins220 (Kinase D-interacting substrate of 220 kDa) is an essential effector of crucial pathways for neuronal survival and differentiation. It is dramatically altered in cancer and in neurological and neurodegenerative disorders, emerging as a regulatory molecule with important functions in human disease. Herein, we discover severe neurogenic deficits and hippocampal-based spatial memory defects accompanied by increased neuroblast death and high loss of newly formed neurons in Kidins220 deficient mice. Mechanistically, we demonstrate that Kidins220-dependent activation of AKT in response to EGF restraints GSK3 activity preventing NSCs apoptosis. We also show that NSCs with Kidins220 can survive with lower concentrations of EGF than the ones lacking this molecule. Hence, Kidins220 levels set a molecular threshold for survival in response to mitogens, allowing adult NSCs growth and expansion. Our study identifies Kidins220 as a key player for sensing the availability of growth factors to sustain adult neurogenesis, uncovering a molecular link that may help paving the way towards neurorepairThis work was funded by grants RYC2014-15991 (MINECO/ESF), SAF2015-67756-R (MCIN/AEI /10.13039/501100011033 and by ERDF “A way of making Europe") and PID2019-104763RB-I00 to EP, PID2020-115218RB-I00 to TI, PID2020-117937GB-I00 to IF, PID2020-115217RB-I00 to MRC, funded by MCIN/AEI/ 10.13039/501100011033; by Centro de Investigación Biomédica en Red de Enfermedades Neurodegenerativas (CIBERNED, Instituto de Salud Carlos III, Spain) and collaborative grants CIBERNED-2015-2/06 and 2018/06 to TI and IF; by PROMETEO/2021/028 of Generalitat Valenciana to IF; by Wellcome Senior Investigator Awards (107116/Z/15/Z and 223022/Z/21/Z) and a UK Dementia Research Institute Foundation award (UKDRI 1005) to GS. ADP was supported by grant FJCI-2014-19673 funded by MCIN/AEI/10.13039/501100011033 and by ESF “Investing in your future”; and a CIBERNED contract; AS-G was supported by a contract associated to PID2020-115218RB-I00 project; EP was supported by a Ramón y Cajal contract (RYC2014-15991, MINECO/ESF), ALB-M by grant FPI BES-2016-078481 associated to SAF2015-67756-R to EP. JP-U was supported by a CIBERNED contract. CLF is recipient of a FPI grant funded by UAM. The cost of this publication has been paid in part by “ERDF A way of making Europe” fundsSpringer NatureDepartamento de Biología MolecularFacultad de Ciencias20232023-08-01research articlehttp://purl.org/coar/resource_type/c_2df8fbb1VoRhttp://purl.org/coar/version/c_970fb48d4fbd8a85info:eu-repo/semantics/articleapplication/pdfhttp://hdl.handle.net/10486/712194https://dx.doi.org/10.1038/s41419-023-05995-7reponame:Biblos-e Archivo. Repositorio Institucional de la UAMinstname:Universidad Autónoma de MadridInglésengopen accesshttp://purl.org/coar/access_right/c_abf2info:eu-repo/semantics/openAccessoai:repositorio.uam.es:10486/7121942026-06-23T12:46:27Z
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