Urothelial organoids originating from Cd49fhigh mouse stem cells display Notch-dependent differentiation capacity

Understanding urothelial stem cell biology and differentiation has been limited by the lack of methods for their unlimited propagation. Here, we establish mouse urothelial organoids that can be maintained uninterruptedly for >1 year. Organoid growth is dependent on EGF and Wnt activators. High CD...

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Autores: Santos, Catarina P, Lapi, Eleonora, Martínez de Villarreal, Jaime, Álvaro-Espinosa, Laura, Fernández-Barral, Asunción, Barbáchano, Antonio, Dominguez, Orlando, Laughney, Ashley M, Megias Vazquez, Diego, Muñoz, Alberto, Real Arribas, Francisco
Tipo de recurso: artículo
Fecha de publicación:2019
País:España
Institución:Instituto de Salud Carlos III (ISCIII)
Repositorio:Repisalud
Idioma:inglés
OAI Identifier:oai:repisalud.isciii.es:20.500.12105/9319
Acceso en línea:http://hdl.handle.net/20.500.12105/9319
Access Level:acceso abierto
Palabra clave:Animals
Cell Differentiation
Cell Line, Tumor
Epidermal Growth Factor
Gene Expression Profiling
Gene Ontology
Gene Regulatory Networks
Humans
Integrin alpha6
Mice, 129 Strain
Mice, Inbred C57BL
Mice, Nude
Mice, Transgenic
Organoids
Receptors, Notch
Single-Cell Analysis
Stem Cells
Urothelium
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spelling Urothelial organoids originating from Cd49fhigh mouse stem cells display Notch-dependent differentiation capacitySantos, Catarina PLapi, EleonoraMartínez de Villarreal, JaimeÁlvaro-Espinosa, LauraFernández-Barral, AsunciónBarbáchano, AntonioDominguez, OrlandoLaughney, Ashley MMegias Vazquez, DiegoMuñoz, AlbertoReal Arribas, FranciscoAnimalsCell DifferentiationCell Line, TumorEpidermal Growth FactorGene Expression ProfilingGene OntologyGene Regulatory NetworksHumansIntegrin alpha6Mice, 129 StrainMice, Inbred C57BLMice, NudeMice, TransgenicOrganoidsReceptors, NotchSingle-Cell AnalysisStem CellsUrotheliumUnderstanding urothelial stem cell biology and differentiation has been limited by the lack of methods for their unlimited propagation. Here, we establish mouse urothelial organoids that can be maintained uninterruptedly for >1 year. Organoid growth is dependent on EGF and Wnt activators. High CD49f/ITGA6 expression features a subpopulation of organoid-forming cells expressing basal markers. Upon differentiation, multilayered organoids undergo reduced proliferation, decreased cell layer number, urothelial program activation, and acquisition of barrier function. Pharmacological modulation of PPARγ and EGFR promotes differentiation. RNA sequencing highlighted genesets enriched in proliferative organoids (i.e. ribosome) and transcriptional networks involved in differentiation, including expression of Wnt ligands and Notch components. Single-cell RNA sequencing (scRNA-Seq) analysis of the organoids revealed five clusters with distinct gene expression profiles. Together, with the use of γ-secretase inhibitors and scRNA-Seq, confirms that Notch signaling is required for differentiation. Urothelial organoids provide a powerful tool to study cell regeneration and differentiation.Nature Publishing GroupMinisterio de Economía y Competitividad (España)Centro de Investigación Biomédica en Red - CIBERONC (Cáncer)Asociación Española Contra el Cáncer20202020-03-2420192019-09-2720192019-09-27journal articlehttp://purl.org/coar/resource_type/c_6501VoRhttp://purl.org/coar/version/c_970fb48d4fbd8a85info:eu-repo/semantics/articleapplication/pdfvideo/quicktimeapplication/pdfapplication/vnd.openxmlformats-officedocument.spreadsheetml.sheetapplication/vnd.openxmlformats-officedocument.spreadsheetml.sheetvideo/quicktimeapplication/pdfapplication/pdfapplication/pdfhttp://hdl.handle.net/20.500.12105/9319reponame:Repisaludinstname:Instituto de Salud Carlos III (ISCIII)Inglésengopen accesshttp://purl.org/coar/access_right/c_abf2Atribución-NoComercial-CompartirIgual 4.0 Internacionalhttp://creativecommons.org/licenses/by-nc-sa/4.0/info:eu-repo/semantics/openAccessoai:repisalud.isciii.es:20.500.12105/93192026-06-12T12:43:37Z
dc.title.none.fl_str_mv Urothelial organoids originating from Cd49fhigh mouse stem cells display Notch-dependent differentiation capacity
title Urothelial organoids originating from Cd49fhigh mouse stem cells display Notch-dependent differentiation capacity
spellingShingle Urothelial organoids originating from Cd49fhigh mouse stem cells display Notch-dependent differentiation capacity
Santos, Catarina P
Animals
Cell Differentiation
Cell Line, Tumor
Epidermal Growth Factor
Gene Expression Profiling
Gene Ontology
Gene Regulatory Networks
Humans
Integrin alpha6
Mice, 129 Strain
Mice, Inbred C57BL
Mice, Nude
Mice, Transgenic
Organoids
Receptors, Notch
Single-Cell Analysis
Stem Cells
Urothelium
title_short Urothelial organoids originating from Cd49fhigh mouse stem cells display Notch-dependent differentiation capacity
title_full Urothelial organoids originating from Cd49fhigh mouse stem cells display Notch-dependent differentiation capacity
title_fullStr Urothelial organoids originating from Cd49fhigh mouse stem cells display Notch-dependent differentiation capacity
title_full_unstemmed Urothelial organoids originating from Cd49fhigh mouse stem cells display Notch-dependent differentiation capacity
title_sort Urothelial organoids originating from Cd49fhigh mouse stem cells display Notch-dependent differentiation capacity
dc.creator.none.fl_str_mv Santos, Catarina P
Lapi, Eleonora
Martínez de Villarreal, Jaime
Álvaro-Espinosa, Laura
Fernández-Barral, Asunción
Barbáchano, Antonio
Dominguez, Orlando
Laughney, Ashley M
Megias Vazquez, Diego
Muñoz, Alberto
Real Arribas, Francisco
author Santos, Catarina P
author_facet Santos, Catarina P
Lapi, Eleonora
Martínez de Villarreal, Jaime
Álvaro-Espinosa, Laura
Fernández-Barral, Asunción
Barbáchano, Antonio
Dominguez, Orlando
Laughney, Ashley M
Megias Vazquez, Diego
Muñoz, Alberto
Real Arribas, Francisco
author_role author
author2 Lapi, Eleonora
Martínez de Villarreal, Jaime
Álvaro-Espinosa, Laura
Fernández-Barral, Asunción
Barbáchano, Antonio
Dominguez, Orlando
Laughney, Ashley M
Megias Vazquez, Diego
Muñoz, Alberto
Real Arribas, Francisco
author2_role author
author
author
author
author
author
author
author
author
author
dc.contributor.none.fl_str_mv Ministerio de Economía y Competitividad (España)
Centro de Investigación Biomédica en Red - CIBERONC (Cáncer)
Asociación Española Contra el Cáncer

dc.subject.none.fl_str_mv Animals
Cell Differentiation
Cell Line, Tumor
Epidermal Growth Factor
Gene Expression Profiling
Gene Ontology
Gene Regulatory Networks
Humans
Integrin alpha6
Mice, 129 Strain
Mice, Inbred C57BL
Mice, Nude
Mice, Transgenic
Organoids
Receptors, Notch
Single-Cell Analysis
Stem Cells
Urothelium
topic Animals
Cell Differentiation
Cell Line, Tumor
Epidermal Growth Factor
Gene Expression Profiling
Gene Ontology
Gene Regulatory Networks
Humans
Integrin alpha6
Mice, 129 Strain
Mice, Inbred C57BL
Mice, Nude
Mice, Transgenic
Organoids
Receptors, Notch
Single-Cell Analysis
Stem Cells
Urothelium
description Understanding urothelial stem cell biology and differentiation has been limited by the lack of methods for their unlimited propagation. Here, we establish mouse urothelial organoids that can be maintained uninterruptedly for >1 year. Organoid growth is dependent on EGF and Wnt activators. High CD49f/ITGA6 expression features a subpopulation of organoid-forming cells expressing basal markers. Upon differentiation, multilayered organoids undergo reduced proliferation, decreased cell layer number, urothelial program activation, and acquisition of barrier function. Pharmacological modulation of PPARγ and EGFR promotes differentiation. RNA sequencing highlighted genesets enriched in proliferative organoids (i.e. ribosome) and transcriptional networks involved in differentiation, including expression of Wnt ligands and Notch components. Single-cell RNA sequencing (scRNA-Seq) analysis of the organoids revealed five clusters with distinct gene expression profiles. Together, with the use of γ-secretase inhibitors and scRNA-Seq, confirms that Notch signaling is required for differentiation. Urothelial organoids provide a powerful tool to study cell regeneration and differentiation.
publishDate 2019
dc.date.none.fl_str_mv 2019
2019-09-27
2019
2019-09-27
2020
2020-03-24
dc.type.none.fl_str_mv journal article
http://purl.org/coar/resource_type/c_6501
VoR
http://purl.org/coar/version/c_970fb48d4fbd8a85
dc.type.openaire.fl_str_mv info:eu-repo/semantics/article
format article
dc.identifier.none.fl_str_mv http://hdl.handle.net/20.500.12105/9319
url http://hdl.handle.net/20.500.12105/9319
dc.language.none.fl_str_mv Inglés
eng
language_invalid_str_mv Inglés
language eng
dc.rights.none.fl_str_mv open access
http://purl.org/coar/access_right/c_abf2
Atribución-NoComercial-CompartirIgual 4.0 Internacional
http://creativecommons.org/licenses/by-nc-sa/4.0/
dc.rights.openaire.fl_str_mv info:eu-repo/semantics/openAccess
rights_invalid_str_mv open access
http://purl.org/coar/access_right/c_abf2
Atribución-NoComercial-CompartirIgual 4.0 Internacional
http://creativecommons.org/licenses/by-nc-sa/4.0/
eu_rights_str_mv openAccess
dc.format.none.fl_str_mv application/pdf
video/quicktime
application/pdf
application/vnd.openxmlformats-officedocument.spreadsheetml.sheet
application/vnd.openxmlformats-officedocument.spreadsheetml.sheet
video/quicktime
application/pdf
application/pdf
application/pdf
dc.publisher.none.fl_str_mv Nature Publishing Group
publisher.none.fl_str_mv Nature Publishing Group
dc.source.none.fl_str_mv reponame:Repisalud
instname:Instituto de Salud Carlos III (ISCIII)
instname_str Instituto de Salud Carlos III (ISCIII)
reponame_str Repisalud
collection Repisalud
repository.name.fl_str_mv
repository.mail.fl_str_mv
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