Generation and validation of a novel multitarget small molecule in glioblastoma

The development of multitarget small molecules (MSMs) has emerged as a powerful strategy for the treatment of multifactorial diseases such as cancer. Glioblastoma is the most prevalent and malignant primary brain tumor in adults, which is characterized by poor prognosis and a high heterogeneity. Cur...

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Autores: Artetxe-Zurutuza, A., Iturrioz-Rodriguez, N., Elizazu, J., Toledano-Pinedo, Mireia, Porro-Pérez, A., De Goñi, I., Elua-Pinin, A., Schäker-Hübner, L., Azkargorta, M., Elortza, F., Lòpez-Muñoz, F., Moncho-Amor, Verónica, Hansen, F. K., Sampron, N., Marco-Contelles, José, Matheu, A.
Tipo de recurso: artículo
Estado:Versión publicada
Fecha de publicación:2025
País:España
Institución:Consejo Superior de Investigaciones Científicas (CSIC)
Repositorio:DIGITAL.CSIC. Repositorio Institucional del CSIC
OAI Identifier:oai:digital.csic.es:10261/387951
Acceso en línea:http://hdl.handle.net/10261/387951
Access Level:acceso abierto
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spelling Generation and validation of a novel multitarget small molecule in glioblastomaArtetxe-Zurutuza, A.Iturrioz-Rodriguez, N.Elizazu, J.Toledano-Pinedo, MireiaPorro-Pérez, A.De Goñi, I.Elua-Pinin, A.Schäker-Hübner, L.Azkargorta, M.Elortza, F.Lòpez-Muñoz, F.Moncho-Amor, VerónicaHansen, F. K.Sampron, N.Marco-Contelles, JoséMatheu, A.The development of multitarget small molecules (MSMs) has emerged as a powerful strategy for the treatment of multifactorial diseases such as cancer. Glioblastoma is the most prevalent and malignant primary brain tumor in adults, which is characterized by poor prognosis and a high heterogeneity. Current standards of treatment present limited effectiveness, as patients develop therapy resistance and recur. In this work, we synthesized and characterized a novel multi-target molecule (named DDI199 or contilistat), which is a polyfunctionalized indole derivative developed by juxtaposing selected pharmacophoric moieties of the parent compounds Contilisant and Vorinostat (SAHA) to act as multifunctional ligands that inhibit histone deacetylases (HDACs), monoamine oxidases (MAOs) and cholinesterases (ChEs), and modulate histamine H3 (H3R) and Sigma 1 Receptor (S1R) receptors. DDI199 exerts high cytotoxic activity in conventional glioblastoma cell lines and patient-derived glioma stem cells in vitro. Importantly, it significantly reduces tumor growth in vivo, both alone and in combination with temozolomide (TMZ). The comparison with SAHA showed higher target specificity and antitumor activity of the new molecule. Transcriptomic and proteomic analyses of patient-derived glioma stem cells revealed a deregulation in cell cycle, DNA remodeling and neurotransmission activity by the treatment with DDI199. In conclusion, our data reveal the efficacy of a novel MSM in glioblastoma pre-clinical setting.A.A-Z received a predoctoral fellowship from the Education Department of the Basque Government (PRE_2020_1_0130). N.I-R is the recipient of a Sara Borrell postdoctoral contract (CD22/00076) and V. M-A by Miguel Servet contract (CP23/ 00111) from Carlos III Institute of Health. LSH wants to gratefully acknowledge experimental support by Philipp Stegen. The authors thank the Neurooncology Committee of the Donostia Hospital and the Animal facility and Pathology Service of Biogipuzkoa Institute for their help. This work was supported by grants from Carlos III Institute of Health and the European Regional Development Fund (PI19/01355, PI22/ 01905, DTS24/00153) and Health Department of the Basque Country (2022333034, 2023333012) to AM, AEI (PID2019-105813RB-C21) and UCJC (MITOPI) (2022) to JMC, and Deutsche Forschungsgemeinschaft (DFG, German Research Foundation) −GRK2873 (494832089) to L.S-H and FK.H.Nature Publishing GroupEusko JaurlaritzaInstituto de Salud Carlos IIIMinisterio de Ciencia e Innovación (España)German Research FoundationConsejo Superior de Investigaciones Científicas [https://ror.org/02gfc7t72]2025202520252025info:eu-repo/semantics/articlehttp://purl.org/coar/resource_type/c_6501Publisher's versioninfo:eu-repo/semantics/publishedVersionhttp://hdl.handle.net/10261/387951reponame:DIGITAL.CSIC. Repositorio Institucional del CSICinstname:Consejo Superior de Investigaciones Científicas (CSIC)Inglés#PLACEHOLDER_PARENT_METADATA_VALUE#info:eu-repo/grantAgreement/AEI/Plan Estatal de Investigación Científica y Técnica y de Innovación 2017-2020/PID2019-105813RB-C21http://dx.doi.org/10.1038/s41419-025-07569-1Síinfo:eu-repo/semantics/openAccessoai:digital.csic.es:10261/3879512026-05-22T06:33:51Z
dc.title.none.fl_str_mv Generation and validation of a novel multitarget small molecule in glioblastoma
title Generation and validation of a novel multitarget small molecule in glioblastoma
spellingShingle Generation and validation of a novel multitarget small molecule in glioblastoma
Artetxe-Zurutuza, A.
title_short Generation and validation of a novel multitarget small molecule in glioblastoma
title_full Generation and validation of a novel multitarget small molecule in glioblastoma
title_fullStr Generation and validation of a novel multitarget small molecule in glioblastoma
title_full_unstemmed Generation and validation of a novel multitarget small molecule in glioblastoma
title_sort Generation and validation of a novel multitarget small molecule in glioblastoma
dc.creator.none.fl_str_mv Artetxe-Zurutuza, A.
Iturrioz-Rodriguez, N.
Elizazu, J.
Toledano-Pinedo, Mireia
Porro-Pérez, A.
De Goñi, I.
Elua-Pinin, A.
Schäker-Hübner, L.
Azkargorta, M.
Elortza, F.
Lòpez-Muñoz, F.
Moncho-Amor, Verónica
Hansen, F. K.
Sampron, N.
Marco-Contelles, José
Matheu, A.
author Artetxe-Zurutuza, A.
author_facet Artetxe-Zurutuza, A.
Iturrioz-Rodriguez, N.
Elizazu, J.
Toledano-Pinedo, Mireia
Porro-Pérez, A.
De Goñi, I.
Elua-Pinin, A.
Schäker-Hübner, L.
Azkargorta, M.
Elortza, F.
Lòpez-Muñoz, F.
Moncho-Amor, Verónica
Hansen, F. K.
Sampron, N.
Marco-Contelles, José
Matheu, A.
author_role author
author2 Iturrioz-Rodriguez, N.
Elizazu, J.
Toledano-Pinedo, Mireia
Porro-Pérez, A.
De Goñi, I.
Elua-Pinin, A.
Schäker-Hübner, L.
Azkargorta, M.
Elortza, F.
Lòpez-Muñoz, F.
Moncho-Amor, Verónica
Hansen, F. K.
Sampron, N.
Marco-Contelles, José
Matheu, A.
author2_role author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
dc.contributor.none.fl_str_mv Eusko Jaurlaritza
Instituto de Salud Carlos III
Ministerio de Ciencia e Innovación (España)
German Research Foundation
Consejo Superior de Investigaciones Científicas [https://ror.org/02gfc7t72]
description The development of multitarget small molecules (MSMs) has emerged as a powerful strategy for the treatment of multifactorial diseases such as cancer. Glioblastoma is the most prevalent and malignant primary brain tumor in adults, which is characterized by poor prognosis and a high heterogeneity. Current standards of treatment present limited effectiveness, as patients develop therapy resistance and recur. In this work, we synthesized and characterized a novel multi-target molecule (named DDI199 or contilistat), which is a polyfunctionalized indole derivative developed by juxtaposing selected pharmacophoric moieties of the parent compounds Contilisant and Vorinostat (SAHA) to act as multifunctional ligands that inhibit histone deacetylases (HDACs), monoamine oxidases (MAOs) and cholinesterases (ChEs), and modulate histamine H3 (H3R) and Sigma 1 Receptor (S1R) receptors. DDI199 exerts high cytotoxic activity in conventional glioblastoma cell lines and patient-derived glioma stem cells in vitro. Importantly, it significantly reduces tumor growth in vivo, both alone and in combination with temozolomide (TMZ). The comparison with SAHA showed higher target specificity and antitumor activity of the new molecule. Transcriptomic and proteomic analyses of patient-derived glioma stem cells revealed a deregulation in cell cycle, DNA remodeling and neurotransmission activity by the treatment with DDI199. In conclusion, our data reveal the efficacy of a novel MSM in glioblastoma pre-clinical setting.
publishDate 2025
dc.date.none.fl_str_mv 2025
2025
2025
2025
dc.type.none.fl_str_mv info:eu-repo/semantics/article
http://purl.org/coar/resource_type/c_6501
Publisher's version
info:eu-repo/semantics/publishedVersion
format article
status_str publishedVersion
dc.identifier.none.fl_str_mv http://hdl.handle.net/10261/387951
url http://hdl.handle.net/10261/387951
dc.language.none.fl_str_mv Inglés
language_invalid_str_mv Inglés
dc.relation.none.fl_str_mv #PLACEHOLDER_PARENT_METADATA_VALUE#
info:eu-repo/grantAgreement/AEI/Plan Estatal de Investigación Científica y Técnica y de Innovación 2017-2020/PID2019-105813RB-C21
http://dx.doi.org/10.1038/s41419-025-07569-1

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