Decapping protein EDC4 regulates DNA repair and phenocopies BRCA1

BRCA1 is a tumor suppressor that regulates DNA repair by homologous recombination. Germline mutations in BRCA1 are associated with increased risk of breast and ovarian cancer and BRCA1 deficient tumors are exquisitely sensitive to poly (ADP-ribose) polymerase (PARP) inhibitors. Therefore, uncovering...

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Autores: Hernández Viedma, Gonzalo|||0000-0002-3048-9607, Ramírez de Haro, Ma. José|||0000-0003-1417-7731, Minguillón Pedreño, Jordi|||0000-0003-2124-8294, Quiles, Francisco, Ruiz de Garibay, G., Aza-Carmona, Miriam|||0000-0003-4448-9541, Bogliolo, Massimo|||0000-0001-8240-7784, Pujol Calvet, Maria Roser|||0000-0003-1840-5455, Prados-Carvajal, Rosario, Fernández-Rodríguez, Juana, García, Nadia, López, Adrià, Gutiérrez-Enríquez, Sara|||0000-0002-1711-6101, Diez, Orland|||0000-0001-7339-0570, Benitez, Javier|||0000-0002-0923-7202, Salinas, Monica, Teule, Alex|||0000-0003-0028-7200, Brunet, Joan|||0000-0003-1945-3512, Radice, Paolo|||0000-0001-6298-4111, Peterlongo, Paolo|||0000-0001-6951-6855, Schindler, Detlev, Huertas, Pablo, Puente, Xose P., Lázaro, Coxi, Pujana, Miguel Angel|||0000-0003-3222-4044, Surralles, Jordi|||0000-0002-4041-7519
Tipo de recurso: artículo
Fecha de publicación:2018
País:España
Institución:Universitat Autònoma de Barcelona
Repositorio:Dipòsit Digital de Documents de la UAB
Idioma:inglés
OAI Identifier:oai:ddd.uab.cat:188030
Acceso en línea:https://ddd.uab.cat/record/188030
https://dx.doi.org/urn:doi:10.1038/s41467-018-03433-3
Access Level:acceso abierto
Palabra clave:Cancer
Double-strand DNA breaks
Genomic instability
RNA metabolism
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oai_identifier_str oai:ddd.uab.cat:188030
network_acronym_str ES
network_name_str España
repository_id_str
dc.title.none.fl_str_mv Decapping protein EDC4 regulates DNA repair and phenocopies BRCA1
title Decapping protein EDC4 regulates DNA repair and phenocopies BRCA1
spellingShingle Decapping protein EDC4 regulates DNA repair and phenocopies BRCA1
Hernández Viedma, Gonzalo|||0000-0002-3048-9607
Cancer
Double-strand DNA breaks
Genomic instability
RNA metabolism
title_short Decapping protein EDC4 regulates DNA repair and phenocopies BRCA1
title_full Decapping protein EDC4 regulates DNA repair and phenocopies BRCA1
title_fullStr Decapping protein EDC4 regulates DNA repair and phenocopies BRCA1
title_full_unstemmed Decapping protein EDC4 regulates DNA repair and phenocopies BRCA1
title_sort Decapping protein EDC4 regulates DNA repair and phenocopies BRCA1
dc.creator.none.fl_str_mv Hernández Viedma, Gonzalo|||0000-0002-3048-9607
Ramírez de Haro, Ma. José|||0000-0003-1417-7731
Minguillón Pedreño, Jordi|||0000-0003-2124-8294
Quiles, Francisco
Ruiz de Garibay, G.
Aza-Carmona, Miriam|||0000-0003-4448-9541
Bogliolo, Massimo|||0000-0001-8240-7784
Pujol Calvet, Maria Roser|||0000-0003-1840-5455
Prados-Carvajal, Rosario
Fernández-Rodríguez, Juana
García, Nadia
López, Adrià
Gutiérrez-Enríquez, Sara|||0000-0002-1711-6101
Diez, Orland|||0000-0001-7339-0570
Benitez, Javier|||0000-0002-0923-7202
Salinas, Monica
Teule, Alex|||0000-0003-0028-7200
Brunet, Joan|||0000-0003-1945-3512
Radice, Paolo|||0000-0001-6298-4111
Peterlongo, Paolo|||0000-0001-6951-6855
Schindler, Detlev
Huertas, Pablo
Puente, Xose P.
Lázaro, Coxi
Pujana, Miguel Angel|||0000-0003-3222-4044
Surralles, Jordi|||0000-0002-4041-7519
author Hernández Viedma, Gonzalo|||0000-0002-3048-9607
author_facet Hernández Viedma, Gonzalo|||0000-0002-3048-9607
Ramírez de Haro, Ma. José|||0000-0003-1417-7731
Minguillón Pedreño, Jordi|||0000-0003-2124-8294
Quiles, Francisco
Ruiz de Garibay, G.
Aza-Carmona, Miriam|||0000-0003-4448-9541
Bogliolo, Massimo|||0000-0001-8240-7784
Pujol Calvet, Maria Roser|||0000-0003-1840-5455
Prados-Carvajal, Rosario
Fernández-Rodríguez, Juana
García, Nadia
López, Adrià
Gutiérrez-Enríquez, Sara|||0000-0002-1711-6101
Diez, Orland|||0000-0001-7339-0570
Benitez, Javier|||0000-0002-0923-7202
Salinas, Monica
Teule, Alex|||0000-0003-0028-7200
Brunet, Joan|||0000-0003-1945-3512
Radice, Paolo|||0000-0001-6298-4111
Peterlongo, Paolo|||0000-0001-6951-6855
Schindler, Detlev
Huertas, Pablo
Puente, Xose P.
Lázaro, Coxi
Pujana, Miguel Angel|||0000-0003-3222-4044
Surralles, Jordi|||0000-0002-4041-7519
author_role author
author2 Ramírez de Haro, Ma. José|||0000-0003-1417-7731
Minguillón Pedreño, Jordi|||0000-0003-2124-8294
Quiles, Francisco
Ruiz de Garibay, G.
Aza-Carmona, Miriam|||0000-0003-4448-9541
Bogliolo, Massimo|||0000-0001-8240-7784
Pujol Calvet, Maria Roser|||0000-0003-1840-5455
Prados-Carvajal, Rosario
Fernández-Rodríguez, Juana
García, Nadia
López, Adrià
Gutiérrez-Enríquez, Sara|||0000-0002-1711-6101
Diez, Orland|||0000-0001-7339-0570
Benitez, Javier|||0000-0002-0923-7202
Salinas, Monica
Teule, Alex|||0000-0003-0028-7200
Brunet, Joan|||0000-0003-1945-3512
Radice, Paolo|||0000-0001-6298-4111
Peterlongo, Paolo|||0000-0001-6951-6855
Schindler, Detlev
Huertas, Pablo
Puente, Xose P.
Lázaro, Coxi
Pujana, Miguel Angel|||0000-0003-3222-4044
Surralles, Jordi|||0000-0002-4041-7519
author2_role author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
author
dc.subject.none.fl_str_mv Cancer
Double-strand DNA breaks
Genomic instability
RNA metabolism
topic Cancer
Double-strand DNA breaks
Genomic instability
RNA metabolism
description BRCA1 is a tumor suppressor that regulates DNA repair by homologous recombination. Germline mutations in BRCA1 are associated with increased risk of breast and ovarian cancer and BRCA1 deficient tumors are exquisitely sensitive to poly (ADP-ribose) polymerase (PARP) inhibitors. Therefore, uncovering additional components of this DNA repair pathway is of extreme importance for further understanding cancer development and therapeutic vulnerabilities. Here, we identify EDC4, a known component of processing-bodies and regulator of mRNA decapping, as a member of the BRCA1-BRIP1-TOPBP1 complex. EDC4 plays a key role in homologous recombination by stimulating end resection at double-strand breaks. EDC4 deficiency leads to genome instability and hypersensitivity to DNA interstrand cross-linking drugs and PARP inhibitors. Lack-of-function mutations in EDC4 were detected in BRCA1/2-mutation-negative breast cancer cases, suggesting a role in breast cancer susceptibility. Collectively, this study recognizes EDC4 with a dual role in decapping and DNA repair whose inactivation phenocopies BRCA1 deficiency.
publishDate 2018
dc.date.none.fl_str_mv 2
2018-01-01
2018
2018-01-01
dc.type.none.fl_str_mv Article
http://purl.org/coar/resource_type/c_6501
VoR
http://purl.org/coar/version/c_970fb48d4fbd8a85
dc.type.openaire.fl_str_mv info:eu-repo/semantics/article
format article
dc.identifier.none.fl_str_mv https://ddd.uab.cat/record/188030
https://dx.doi.org/urn:doi:10.1038/s41467-018-03433-3
url https://ddd.uab.cat/record/188030
https://dx.doi.org/urn:doi:10.1038/s41467-018-03433-3
dc.language.none.fl_str_mv Inglés
eng
language_invalid_str_mv Inglés
language eng
dc.relation.none.fl_str_mv European Commission https://doi.org/10.13039/501100000780 305421
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 SAF2015-64152-R
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 SAF2013-45836-R
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 SAF2012-31881
Ministerio de Sanidad y Consumo https://doi.org/10.13039/501100003329 CB06/07/0023
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PIE13/00022
Ministerio de Ciencia e Innovación https://doi.org/10.13039/501100004837 CP10/00617
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI10/01422
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI12/02585
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI13/00285
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI15/00854
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI16/00563
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI16/01218
Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 RD12/0036/0008
Agència de Gestió d'Ajuts Universitaris i de Recerca https://doi.org/10.13039/501100003030 2014/SGR-364
Agència de Gestió d'Ajuts Universitaris i de Recerca https://doi.org/10.13039/501100003030 2014/SGR-338
dc.rights.none.fl_str_mv open access
http://purl.org/coar/access_right/c_abf2
https://creativecommons.org/licenses/by/4.0/
dc.rights.openaire.fl_str_mv info:eu-repo/semantics/openAccess
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dc.source.none.fl_str_mv reponame:Dipòsit Digital de Documents de la UAB
instname:Universitat Autònoma de Barcelona
instname_str Universitat Autònoma de Barcelona
reponame_str Dipòsit Digital de Documents de la UAB
collection Dipòsit Digital de Documents de la UAB
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spelling Decapping protein EDC4 regulates DNA repair and phenocopies BRCA1Hernández Viedma, Gonzalo|||0000-0002-3048-9607Ramírez de Haro, Ma. José|||0000-0003-1417-7731Minguillón Pedreño, Jordi|||0000-0003-2124-8294Quiles, FranciscoRuiz de Garibay, G.Aza-Carmona, Miriam|||0000-0003-4448-9541Bogliolo, Massimo|||0000-0001-8240-7784Pujol Calvet, Maria Roser|||0000-0003-1840-5455Prados-Carvajal, RosarioFernández-Rodríguez, JuanaGarcía, NadiaLópez, AdriàGutiérrez-Enríquez, Sara|||0000-0002-1711-6101Diez, Orland|||0000-0001-7339-0570Benitez, Javier|||0000-0002-0923-7202Salinas, MonicaTeule, Alex|||0000-0003-0028-7200Brunet, Joan|||0000-0003-1945-3512Radice, Paolo|||0000-0001-6298-4111Peterlongo, Paolo|||0000-0001-6951-6855Schindler, DetlevHuertas, PabloPuente, Xose P.Lázaro, CoxiPujana, Miguel Angel|||0000-0003-3222-4044Surralles, Jordi|||0000-0002-4041-7519CancerDouble-strand DNA breaksGenomic instabilityRNA metabolismBRCA1 is a tumor suppressor that regulates DNA repair by homologous recombination. Germline mutations in BRCA1 are associated with increased risk of breast and ovarian cancer and BRCA1 deficient tumors are exquisitely sensitive to poly (ADP-ribose) polymerase (PARP) inhibitors. Therefore, uncovering additional components of this DNA repair pathway is of extreme importance for further understanding cancer development and therapeutic vulnerabilities. Here, we identify EDC4, a known component of processing-bodies and regulator of mRNA decapping, as a member of the BRCA1-BRIP1-TOPBP1 complex. EDC4 plays a key role in homologous recombination by stimulating end resection at double-strand breaks. EDC4 deficiency leads to genome instability and hypersensitivity to DNA interstrand cross-linking drugs and PARP inhibitors. Lack-of-function mutations in EDC4 were detected in BRCA1/2-mutation-negative breast cancer cases, suggesting a role in breast cancer susceptibility. Collectively, this study recognizes EDC4 with a dual role in decapping and DNA repair whose inactivation phenocopies BRCA1 deficiency. 22018-01-0120182018-01-01Articlehttp://purl.org/coar/resource_type/c_6501VoRhttp://purl.org/coar/version/c_970fb48d4fbd8a85info:eu-repo/semantics/articleapplication/pdfhttps://ddd.uab.cat/record/188030https://dx.doi.org/urn:doi:10.1038/s41467-018-03433-3reponame:Dipòsit Digital de Documents de la UABinstname:Universitat Autònoma de BarcelonaInglésengEuropean Commission https://doi.org/10.13039/501100000780 305421Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 SAF2015-64152-RMinisterio de Economía y Competitividad https://doi.org/10.13039/501100003329 SAF2013-45836-RMinisterio de Economía y Competitividad https://doi.org/10.13039/501100003329 SAF2012-31881Ministerio de Sanidad y Consumo https://doi.org/10.13039/501100003329 CB06/07/0023Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PIE13/00022Ministerio de Ciencia e Innovación https://doi.org/10.13039/501100004837 CP10/00617Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI10/01422Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI12/02585Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI13/00285Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI15/00854Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI16/00563Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 PI16/01218Ministerio de Economía y Competitividad https://doi.org/10.13039/501100003329 RD12/0036/0008Agència de Gestió d'Ajuts Universitaris i de Recerca https://doi.org/10.13039/501100003030 2014/SGR-364Agència de Gestió d'Ajuts Universitaris i de Recerca https://doi.org/10.13039/501100003030 2014/SGR-338open accesshttp://purl.org/coar/access_right/c_abf2Aquest document està subjecte a una llicència d'ús Creative Commons. Es permet la reproducció total o parcial, la distribució, la comunicació pública de l'obra i la creació d'obres derivades, fins i tot amb finalitats comercials, sempre i quan es reconegui l'autoria de l'obra original.https://creativecommons.org/licenses/by/4.0/info:eu-repo/semantics/openAccessoai:ddd.uab.cat:1880302026-06-06T12:50:31Z
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