Incomplete Penetrance and Variable Expressivity: Hallmarks in Channelopathies Associated with Sudden Cardiac Death

Sudden cardiac death is defined as an unexpected decease of cardiac origin. In individuals under 35 years old, most of these deaths are due to familial arrhythmogenic syndromes of genetic origin, also known as channelopathies. These familial cardiac syndromes commonly follow an autosomal dominant pa...

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Detalles Bibliográficos
Autores: Coll Vidal, Mònica, Perez-Serra, Alexandra, Matés Ramírez, Jesús, Olmo, Bernat del, Puigmulé, Marta, Fernández-Falgueras, Anna, Iglesias, Anna, Picó, Ferran, López López, Laura, Brugada, Ramon, Campuzano Larrea, Oscar
Tipo de recurso: artículo
Estado:Versión publicada
Fecha de publicación:2017
País:España
Institución:Varias* (Consorci de Biblioteques Universitáries de Catalunya, Centre de Serveis Científics i Acadèmics de Catalunya)
Repositorio:Recercat. Dipósit de la Recerca de Catalunya
OAI Identifier:oai:recercat.cat:10256/15875
Acceso en línea:http://hdl.handle.net/10256/15875
Access Level:acceso abierto
Palabra clave:Mort sobtada
Sudden death
Cor -- Malalties -- Aspectes genètics
Heart -- Diseases -- Genetic aspects
Malalties congènites
Genetic disorders
Genètica mèdica
Medical genetics
Descripción
Sumario:Sudden cardiac death is defined as an unexpected decease of cardiac origin. In individuals under 35 years old, most of these deaths are due to familial arrhythmogenic syndromes of genetic origin, also known as channelopathies. These familial cardiac syndromes commonly follow an autosomal dominant pattern of inheritance. Diagnosis, however, can be difficult, mainly due to incomplete penetrance and variable expressivity, which are hallmarks in these syndromes. The clinical manifestation of these diseases can range from asymptomatic to syncope but sudden death can sometimes be the first symptom of disease. Early identification of at-risk individuals is crucial to prevent a lethal episode. In this review, we will focus on the genetic basis of channelopathies and the effect of genetic and non-genetic modifiers on their phenotypes