Results of a phase 1 study of the oncolytic adenovirus DNX-2401 with radiotherapy for newly diagnosed diffuse intrinsic pontine glioma (DIPG)

Background: A Phase 1, single center study is ongoing to evaluate the conditionally replicative oncolytic adenovirus, DNX-2401 (tasadenoturev), followed by radiotherapy (RT) in pediatric patients with newly diagnosed diffuse intrinsic pontine glioma (DIPG). Methods: Patients 1–18 years with newly di...

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Autores: Garcia-Moure, M. (Marc)|||/items/9741d07b-2525-4e98-9bfc-93fc3e869273, Gallego-Perez-Larraya, J. (Jaime)|||/items/8a92f20a-1e24-427d-8da0-ace4eba5620d, Patiño-García, A. (Ana)|||/items/d68c74f1-df22-4e04-9b77-9cf48fd87b46, Gonzalez-Huarriz, M. (Marisol)|||/items/00a6d7fb-7851-4264-bdfd-9172d60bc40b, Jones, C. (Chris)|||/items/8069bf34-1a1d-48aa-99ce-9d3b1ef10f96, MacKay, A. (Alan)|||/items/9f9c8e0b-58b9-4966-8115-777f322f1e7c, Lugt, J. (Jasper) van der|||/items/aa7268fe-862c-4c5c-9dde-4497396501fa, Hulleman, E. (Esther)|||/items/a1980a44-797b-4ab8-b54a-af4c380abbcb, Andrea, C.E. (Carlos Eduardo) de|||/items/e487698b-8d56-4c3e-8cba-40e33c78083a, Astigarraga, I. (Itziar)|||/items/5005a5cd-b2dd-4dc5-84ad-6a7a8a904b50, García-Ariza, M. (Miguel)|||/items/1f0dd89d-c5fd-4b9d-b143-770c9fb79872, Lopez-Ibor, B. (Blanca)|||/items/3392cdd5-6e55-4059-a592-2affcbaf5e8a, Villalba-Esparza, M. (María)|||/items/203ea86e-61c4-420d-b975-6c7d647bc07e, Lang, F.F. (Frederick F.)|||/items/d081bc57-0a6d-4759-a1fa-0692bd8efe73, Fueyo, J. (Juan)|||/items/a4e5ff79-2565-4461-ab26-34868ff5ff4d, Gomez-Manzano, C. (Candelaria)|||/items/5e8d7495-6be8-46e1-8303-cfd722d30166, Dobbs, J. (Jessica)|||/items/3b2faecf-6f73-4a79-983e-47f0b147c024, Diez-Valle, R. (Ricardo)|||/items/6d489f5e-42e6-4828-9da6-355fb32be7ae, Alonso-Roldán, M.M. (Marta María)|||/items/b912e21e-f895-4efe-bc4c-de1ca8f36c37, Tejada-Solis, S. (Sonia)|||/items/d8fe98eb-18a3-4c6c-b25e-e228767f65e7
Tipo de recurso: artículo
Fecha de publicación:2021
País:España
Institución:Universidad de Navarra
Repositorio:Dadun. Depósito Académico Digital de la Universidad de Navarra
Idioma:inglés
OAI Identifier:oai:dadun.unav.edu:10171/115583
Acceso en línea:https://hdl.handle.net/10171/115583
Access Level:acceso abierto
Palabra clave:DNX-2401
Oncolytic adenovirus
Pediatric patients
Diffuse Intrinsic Pontine Gliomas (DIPG)
Descripción
Sumario:Background: A Phase 1, single center study is ongoing to evaluate the conditionally replicative oncolytic adenovirus, DNX-2401 (tasadenoturev), followed by radiotherapy (RT) in pediatric patients with newly diagnosed diffuse intrinsic pontine glioma (DIPG). Methods: Patients 1–18 years with newly diagnosed DIPG with no prior treatment, Lansky/Karnofsky performance score ≥ 70, and adequate organ function were enrolled. A tumor biopsy was performed followed by a single intratumoral injection of 1e10-5e10 virus particles (vp) DNX-2401. Conventional radiotherapy was initiated within 1 month of DNX-2401 administration. Results. Enrolled subjects (n=12) had a median age of 9 (range 3–18) and performance scores of 90–100 (n=4; 33%) or 70–80 (n=8; 67%). As part of a dose escalation design, subjects were treated with 1e10 vp (n=4) or 5e10 vp DNX-2401 (n=8), which was then followed by standard RT in 11 of 12 subjects (92%). No dose-limiting toxicities were observed and the treatment regimen was well-tolerated. Adverse events (AEs) have been primarily mild to moderate and consistent with underlying disease. The most commonly reported AEs (≥ 5 subjects), regardless of study drug relationship, include headache, asthenia, vomiting, anemia, leukocytosis, and fever. Two SAEs have been reported including grade 3 lymphopenia and grade 3 abdominal pain. Tumor reductions have been observed and efficacy evaluations are ongoing. As of 09Dec2020, 12-month survival (OS-12) was 71% and 4 of 12 patients had survived > 20 months. Four subjects continue to be followed for survival. Correlative analysis of tumor biopsy and peripheral samples is ongoing. Conclusions: DNX-2401 followed by RT can be safely administered to pediatric subjects with newly diagnosed DIPG; clinical activity and preliminary survival are encouraging.