Neuregulin-1 promotes functional improvement by enhancing collateral sprouting in SOD1G93A ALS mice and after partial muscle denervation

Amyotrophic lateral sclerosis (ALS) is a neurodegenerative disease characterized by progressive degeneration of motoneurons, which is preceded by loss of neuromuscular connections in a "dying back" process. Neuregulin-1 (Nrg1) is a neurotrophic factor essential for the development and main...

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Detalhes bibliográficos
Autores: Mancuso, Renzo, Martínez Muriana, Anna|||0000-0002-8645-1317, Leiva-Rodríguez, Tatiana|||0000-0003-0359-0045, Gregorio Martínez, David, Ariza, Lorena, Morell, Marta, Esteban-Pérez, Jesús, García-Redondo, Alberto, Calvo, Ana Cristina|||0000-0001-5193-7782, Atencia-Cibreiro, Gabriela, Corfas, Gabriel, Osta, Rosario|||0000-0001-5687-6704, Bosch i Merino, Assumpció|||0000-0002-7205-2796, Navarro, X. (Xavier)|||0000-0001-9849-902X
Formato: artículo
Fecha de publicación:2016
País:España
Recursos:Universitat Autònoma de Barcelona
Repositorio:Dipòsit Digital de Documents de la UAB
Idioma:inglés
OAI Identifier:oai:ddd.uab.cat:166290
Acesso em linha:https://ddd.uab.cat/record/166290
https://dx.doi.org/urn:doi:10.1016/j.nbd.2016.07.023
Access Level:acceso abierto
Palavra-chave:Neuregulin-1
Amyotrophic lateral sclerosis
Neuromuscular junction
Motoneuron
Collateral sprouting
Descrição
Resumo:Amyotrophic lateral sclerosis (ALS) is a neurodegenerative disease characterized by progressive degeneration of motoneurons, which is preceded by loss of neuromuscular connections in a "dying back" process. Neuregulin-1 (Nrg1) is a neurotrophic factor essential for the development and maintenance of neuromuscular junctions, and Nrg1 receptor ErbB4 loss-of-function mutations have been reported as causative for ALS. Our main goal was to investigate the role of Nrg1 type I (Nrg1-I) in SOD1G93A mice muscles. We overexpressed Nrg1-I by means of an adeno-associated viral (AAV) vector, and investigated its effect by means of neurophysiological techniques assessing neuromuscular function, as well as molecular approaches (RT-PCR, western blot, immunohistochemistry, ELISA) to determine the mechanisms underlying Nrg1-I action. AAV-Nrg1-I intramuscular administration promoted motor axon collateral sprouting by acting on terminal Schwann cells, preventing denervation of the injected muscles through Akt and ERK1/2 pathways. We further used a model of muscle partial denervation by transecting the L4 spinal nerve. AAV-Nrg1-I intramuscular injection enhanced muscle reinnervation by collateral sprouting, whereas administration of lapatinib (ErbB receptor inhibitor) completely blocked it. We demonstrated that Nrg1-I plays a crucial role in the collateral reinnervation process, opening a new window for developing novel ALS therapies for functional recovery rather than preservation.