Two new cases of brazilian boys presenting a Rett-like phenotype due to FOXG1: case report and literature review

Rett syndrome (RTT) is a rare neurodevelopmental disorder usually affecting females. Most typical forms of RTT patients are hemizygous for pathogenic variants in  MECP2.  FOXG1 syndrome is a rare and severe neurodevelopmental disorder with a broad spectrum of clinical features whic...

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Detalles Bibliográficos
Autores: Braga, Vitor Lucas Lopes, Pinheiro, Marcelo de Almeida, Mariano, Tamiris Carneiro, Gomes, Gustavo Rodrigues Ferreira, Marques, Erlane Ribeiro, Pessoa, Andre Luiz Santos
Tipo de recurso: artículo
Estado:Versión publicada
Fecha de publicación:2023
País:Brasil
Institución:Instituto Superior de Educação Vera Cruz (VeraCruz)
Repositorio:Revista Veras
Idioma:inglés
OAI Identifier:oai:ojs2.ojs.brazilianjournals.com.br:article/60699
Acceso en línea:https://ojs.brazilianjournals.com.br/ojs/index.php/BRJD/article/view/60699
Access Level:acceso abierto
Palabra clave:rett syndrome
neurodevelopmental disorders
epilepsy
FOXG1
Descripción
Sumario:Rett syndrome (RTT) is a rare neurodevelopmental disorder usually affecting females. Most typical forms of RTT patients are hemizygous for pathogenic variants in  MECP2.  FOXG1 syndrome is a rare and severe neurodevelopmental disorder with a broad spectrum of clinical features which could be described as RTT-like.  In this paper we describe two non related patients who presented with developmental delay, microcephaly and hyperkinetic movements. One of them had epilepsy. Diagnosis was made by exome analysis and highlights an uncommon differential diagnosis in developmental delay in children.