Sixteen novel hemophilia A causative mutations in the first Argentinian series of severe molecular defects

Hemophilia A (HA) is caused by heterogeneous mutations in the factor VIII gene (F8). This paper reports 16 novel small F8-mutations and rearrangements in a series of 80 Argentinian families with severe-HA. Using an updated scheme for F8-analysis, we found 37 F8-inversions (46%), 10 large deletions (...

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Detalles Bibliográficos
Autores: Rossetti, Liliana Carmen, Radic, Claudia Pamela, Candela, Miguel, Pérez Bianco, Raúl, De Tezanos Pinto, Miguel, Goodeve, Anne, Larripa, Irene Beatriz, de Brasi, Carlos Daniel
Tipo de recurso: artículo
Estado:Versión publicada
Fecha de publicación:2007
País:Argentina
Institución:Consejo Nacional de Investigaciones Científicas y Técnicas
Repositorio:CONICET Digital (CONICET)
Idioma:inglés
OAI Identifier:oai:ri.conicet.gov.ar:11336/55955
Acceso en línea:http://hdl.handle.net/11336/55955
Access Level:acceso abierto
Palabra clave:F8
Hema
Mutation Characterization
Severe Phenotype
https://purl.org/becyt/ford/3.1
https://purl.org/becyt/ford/3
Descripción
Sumario:Hemophilia A (HA) is caused by heterogeneous mutations in the factor VIII gene (F8). This paper reports 16 novel small F8-mutations and rearrangements in a series of 80 Argentinian families with severe-HA. Using an updated scheme for F8-analysis, we found 37 F8-inversions (46%), 10 large deletions (13%), 13 small ins/del (16%), 7 nonsense (9%) and 8 missense mutations (10%), including 4 new ones (p.T233K, p.W1942R, p.L2297P and p.L2301S). The potential changes leading to severe-HA of these latter mutations were suggested by bioinformatics. The F8-mutation was characterised in 76 families (95%). They received genetic counselling and precise information about treatment design. ©2007 Ferrata Storti Foundation.