Epigenetic inactivation of the splicing RNA-binding protein CELF2 in human breast cancer

Human tumors show altered patterns of protein isoforms that can be related to the dysregulation of messenger RNA alternative splicing also observed in transformed cells. Although somatic mutations in core spliceosome components and their associated factors have been described in some cases, almost n...

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Detalles Bibliográficos
Autores: Piqué, Laia, Martinez de Paz, A., Piñeyro, David|||0000-0001-5633-3339, Martínez Cardús, Anna|||0000-0002-3937-8794, Castro de Moura, Manuel|||0000-0002-8488-5306, Llinàs-Arias, Pere|||0000-0002-3666-0532, Setien, F., Gómez-Miragaya, Jorge|||0000-0003-1801-4681, González-Suárez, Eva|||0000-0003-0858-8171, Sigurdsson, S.|||0000-0002-5284-0058, Jonasson, J. G., Villanueva, Alberto|||0000-0001-5164-0006, Vidal, A., Davalos, Veronica|||0000-0003-4077-5137, Esteller, M.|||0000-0003-4490-6093
Tipo de recurso: artículo
Fecha de publicación:2019
País:España
Institución:Universitat Autònoma de Barcelona
Repositorio:Dipòsit Digital de Documents de la UAB
Idioma:inglés
OAI Identifier:oai:ddd.uab.cat:236890
Acceso en línea:https://ddd.uab.cat/record/236890
https://dx.doi.org/urn:doi:10.1038/s41388-019-0936-x
Access Level:acceso abierto
Palabra clave:Breast Neoplasms
CELF Proteins
DNA Methylation
Epigenesis, Genetic
Female
Gene Expression Regulation, Neoplastic
Humans
Nerve Tissue Proteins
RNA Splicing
Spliceosomes
Tumor Cells, Cultured
Descripción
Sumario:Human tumors show altered patterns of protein isoforms that can be related to the dysregulation of messenger RNA alternative splicing also observed in transformed cells. Although somatic mutations in core spliceosome components and their associated factors have been described in some cases, almost nothing is known about the contribution of distorted epigenetic patterns to aberrant splicing. Herein, we show that the splicing RNA-binding protein CELF2 is targeted by promoter hypermethylation-associated transcriptional silencing in human cancer. Focusing on the context of breast cancer, we also demonstrate that CELF2 restoration has growth-inhibitory effects and that its epigenetic loss induces an aberrant downstream pattern of alternative splicing, affecting key genes in breast cancer biology such as the autophagy factor ULK1 and the apoptotic protein CARD10. Furthermore, the presence of CELF2 hypermethylation in the clinical setting is associated with shorter overall survival of the breast cancer patients carrying this epigenetic lesion.